MASTL

Chr 10

microtubule associated serine/threonine kinase like

Also known as: GREATWALL, GW, GWL, MAST-L, THC2

This gene encodes a serine/threonine kinase that regulates mitosis entry and maintenance by promoting protein phosphatase 2A inactivation during M phase, and may be involved in megakaryocyte differentiation. Mutations cause autosomal dominant thrombocytopenia-2, a bleeding disorder affecting platelet production. The gene shows minimal constraint against loss-of-function variants (pLI near zero), suggesting haploinsufficiency is unlikely to be lethal.

Summary from RefSeq, UniProt
Research Assistant →
0
Active trials
12
Pubs (1 yr)
12
P/LP submissions
0%
P/LP missense
0.95
LOEUF
DN
Mechanism· predicted
Clinical SummaryMASTL
🧬
Gene-Disease Validity (ClinGen)
thrombocytopenia · ADLimited

Limited evidence — not for standalone diagnostic reporting

Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.
📋
ClinVar Variants
12 unique Pathogenic / Likely Pathogenic· 140 VUS of 254 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
0.95LOEUF
pLI 0.000
Z-score 1.81
OE 0.68 (0.490.95)
Tolerant

Typical tolerance to LoF variation

Missense Constraint
0.50Z-score
OE missense 0.93 (0.861.01)
428 obs / 458.4 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.68 (0.490.95)
00.351.4
Missense OE0.93 (0.861.01)
00.61.4
Synonymous OE0.87
01.21.6
LoF obs/exp: 25 / 36.9Missense obs/exp: 428 / 458.4Syn Z: 1.37
DN
0.6453th %ile
GOF
0.3987th %ile
LOF
0.4627th %ile

The highest-scoring mechanism for this gene is dominant-negative.

DNprediction above median

Note: In-silico variant effect predictors (SIFT, PolyPhen, REVEL, CADD) may underestimate pathogenicity of missense variants in genes with GOF or DN mechanisms. Consider functional evidence and clinical context.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

254 submitted variants in ClinVar

Classification Summary

Pathogenic11
Likely Pathogenic1
VUS140
Likely Benign37
Benign47
Conflicting3
11
Pathogenic
1
Likely Pathogenic
140
VUS
37
Likely Benign
47
Benign
3
Conflicting

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
0
0
11
0
11
Likely Pathogenic
0
0
1
0
1
VUS
2
118
14
6
140
Likely Benign
0
17
7
13
37
Benign
0
10
34
3
47
Conflicting
3
Total21456722239

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

MASTL · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
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