MAPKAP1

Chr 9

MAPK associated protein 1

Also known as: JC310, MIP1, SIN1, SIN1b, SIN1g

The protein functions as a component of the mechanistic target of rapamycin complex 2 (mTORC2), serving as a substrate adapter that recognizes and binds AGC protein kinase family members for phosphorylation by mTOR, thereby transducing growth factor signals to pathways controlling proliferation, cytoskeletal organization, and metabolism. Loss-of-function mutations in MAPKAP1 are predicted to cause disease through haploinsufficiency, as indicated by the extremely high pLI score (0.9999) and low LOEUF score (0.153), though specific neurogenetic disorders associated with this gene have not yet been characterized. The inheritance pattern and clinical phenotype remain to be defined as this represents an emerging disease gene.

OMIMResearchSummary from RefSeq, UniProt, Mechanism
LOFmechanismLOEUF 0.15
Clinical SummaryMAPKAP1
Population Constraint (gnomAD)
Highly constrained gene — heterozygous loss-of-function variants are very rare in the population (pLI 1.00). One damaged copy is likely sufficient to cause disease.

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

LoF intolerant — likely haploinsufficient
LoF Constraint
0.15LOEUF
pLI 1.000
Z-score 4.99
OE 0.03 (0.010.15)
Highly constrained

Highly LoF-intolerant (top ~10% of genes)

Missense Constraint
2.83Z-score
OE missense 0.54 (0.480.62)
164 obs / 302.4 exp
Mild constraint

Moderately missense-constrained (top ~2.5%)

Observed / Expected Ratios
LoF OE0.03 (0.010.15)
00.351.4
Missense OE0.54 (0.480.62)
00.61.4
Synonymous OE0.91
01.21.6
LoF obs/exp: 1 / 31.0Missense obs/exp: 164 / 302.4Syn Z: 0.78
DN
0.3097th %ile
GOF
0.3590th %ile
LOF
0.72top 10%

The highest-scoring mechanism for this gene is loss-of-function (haploinsufficiency).

LOFprediction above median · LOEUF 0.15

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312. Mechanism ranking also informed by gnomAD constraint, ClinVar, and ClinGen data.

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

MAPKAP1 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
Open Research Assistant →
Key Publications
Landmark & review papers · by relevance
PubMed
Top 5 results · since 2015Search PubMed ↗