MAP7D1

Chr 1

MAP7 domain containing 1

Also known as: PARCC1, RPRC1

MAP7D1 encodes a microtubule-stabilizing protein that controls cell motility and neurite outgrowth by maintaining acetylated stable microtubules. Mutations cause autosomal recessive neurodevelopmental disorders with intellectual disability and developmental delay. The gene is highly constrained against loss-of-function variants, indicating intolerance to protein-truncating mutations.

OMIMResearchSummary from RefSeq, UniProt
LOFmechanismLOEUF 0.29
Clinical SummaryMAP7D1
Population Constraint (gnomAD)
Highly constrained gene — heterozygous loss-of-function variants are very rare in the population (pLI 0.99). One damaged copy is likely sufficient to cause disease.
📋
ClinVar Variants
8 unique Pathogenic / Likely Pathogenic· 147 VUS of 188 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

LoF intolerant — likely haploinsufficient
LoF Constraint
0.29LOEUF
pLI 0.992
Z-score 5.06
OE 0.15 (0.080.29)
Highly constrained

Highly LoF-intolerant (top ~10% of genes)

Missense Constraint
1.00Z-score
OE missense 0.88 (0.810.95)
449 obs / 512.8 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.15 (0.080.29)
00.351.4
Missense OE0.88 (0.810.95)
00.61.4
Synonymous OE0.96
01.21.6
LoF obs/exp: 6 / 40.9Missense obs/exp: 449 / 512.8Syn Z: 0.49
DN
0.3991th %ile
GOF
0.4183th %ile
LOF
0.77top 5%

The highest-scoring mechanism for this gene is loss-of-function (haploinsufficiency).

LOFprediction above median · LOEUF 0.29

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312. Mechanism ranking also informed by gnomAD constraint, ClinVar, and ClinGen data.

ClinVar Variant Classifications

188 submitted variants in ClinVar

Classification Summary

Pathogenic6
Likely Pathogenic2
VUS147
Likely Benign6
Benign3
6
Pathogenic
2
Likely Pathogenic
147
VUS
6
Likely Benign
3
Benign

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
0
0
6
0
6
Likely Pathogenic
0
0
2
0
2
VUS
0
142
5
0
147
Likely Benign
0
4
0
2
6
Benign
0
2
0
1
3
Total0148133164

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

MAP7D1 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
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Full-Text Mentions
NLP-detected gene mentions in article bodies · via PubTator3
PubTator3
Top 3 full-text resultsSearch PubTator3 ↗