MANBA

Chr 4AR

mannosidase beta

Also known as: MANB1

This gene encodes a lysosomal exoglycosidase that cleaves beta-linked mannose residues from N-linked glycoprotein oligosaccharides, serving as the final enzyme in the oligosaccharide catabolism pathway. Mutations cause beta-mannosidosis, an autosomal recessive lysosomal storage disease with a wide spectrum of neurological involvement. The gene shows low constraint to loss-of-function variation (pLI near zero), consistent with its recessive inheritance pattern.

OMIMResearchSummary from RefSeq, OMIM, UniProt
LOFmechanismARLOEUF 0.961 OMIM phenotype
Clinical SummaryMANBA
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Gene-Disease Validity (ClinGen)
beta-mannosidosis · ARDefinitive

Definitive — sufficient evidence for diagnostic panels

Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
0.96LOEUF
pLI 0.000
Z-score 1.75
OE 0.73 (0.560.96)
Tolerant

Typical tolerance to LoF variation

Missense Constraint
0.05Z-score
OE missense 0.99 (0.921.07)
468 obs / 471.0 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.73 (0.560.96)
00.351.4
Missense OE0.99 (0.921.07)
00.61.4
Synonymous OE0.96
01.21.6
LoF obs/exp: 35 / 48.1Missense obs/exp: 468 / 471.0Syn Z: 0.36
Curated Mechanism (G2P)Gene2Phenotype (DDG2P) ↗
definitiveMANBA-related lysosomal beta-mannosidosisLOFAR

Predictions shown for reference only — model trained on dominant genes, not applicable to AR conditions.

DN
0.6259th %ile
GOF
0.6051th %ile
LOF
0.2679th %ile

The Badonyi & Marsh prediction model was trained exclusively on dominant disease genes. Predictions are not reliable for genes with autosomal recessive inheritance and are shown at reduced opacity for reference only.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

MANBA · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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Recent Gene-Specific Literature
Gene in title · MEDLINE · newest first
Europe PMC