LURAP1

Chr 1

leucine rich adaptor protein 1

Also known as: C1orf190, LRAP35a, LRP35A

The protein activates the canonical NF-kappa-B pathway to drive pro-inflammatory cytokine production and promotes dendritic cell antigen presentation, while also regulating actomyosin assembly crucial for cell migration through interactions with MYO18A and CDC42BPA/CDC42BPB. Based on current databases, no established human disease associations have been reported for LURAP1 mutations. The gene shows tolerance to loss-of-function variation (pLI 0.01, LOEUF 1.18), suggesting haploinsufficiency is unlikely to cause disease.

OMIMResearchSummary from RefSeq, UniProt
MultiplemechanismLOEUF 1.18
Clinical SummaryLURAP1
Population Constraint (gnomAD)
Low constraint (pLI 0.01) — loss-of-function variants are relatively tolerated in the population.

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.18LOEUF
pLI 0.012
Z-score 1.24
OE 0.52 (0.251.18)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
0.34Z-score
OE missense 0.92 (0.791.06)
125 obs / 136.3 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.52 (0.251.18)
00.351.4
Missense OE0.92 (0.791.06)
00.61.4
Synonymous OE0.91
01.21.6
LoF obs/exp: 4 / 7.7Missense obs/exp: 125 / 136.3Syn Z: 0.51
DN
0.7036th %ile
GOF
0.72top 25%
LOF
0.4136th %ile

This gene has evidence for multiple mechanisms of pathogenicity (gain-of-function and dominant-negative). Both the Badonyi & Marsh prediction and the broader genomic evidence point to gain-of-function as the predominant mechanism. Different variants in this gene may act through different mechanisms — interpret in context of the specific variant.

GOFprediction above median
DNprediction above median

Note: In-silico variant effect predictors (SIFT, PolyPhen, REVEL, CADD) may underestimate pathogenicity of missense variants in genes with GOF or DN mechanisms. Consider functional evidence and clinical context.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

LURAP1 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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