LSM10

Chr 1

LSM10, U7 small nuclear RNA associated

Also known as: MST074, MSTP074

LSM10 encodes a protein that binds U7 snRNA and functions in the U7 snRNP complex required for histone 3'-end processing and cell cycle progression from G1 to S phases. Mutations in LSM10 cause microcephaly with or without chorioretinopathy, lymphedema, or mental retardation (MCLMR), an autosomal recessive disorder presenting with primary microcephaly and variable additional features including intellectual disability and ocular abnormalities. The gene shows tolerance to loss-of-function variation with a low probability of haploinsufficiency (pLI = 0.004).

OMIMResearchSummary from RefSeq, UniProt
LOEUF 1.91
Clinical SummaryLSM10
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.
📋
ClinVar Variants
8 unique Pathogenic / Likely Pathogenic· 20 VUS of 31 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.91LOEUF
pLI 0.004
Z-score -0.43
OE 1.31 (0.521.91)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
0.47Z-score
OE missense 0.86 (0.711.04)
72 obs / 84.1 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE1.31 (0.521.91)
00.351.4
Missense OE0.86 (0.711.04)
00.61.4
Synonymous OE1.07
01.21.6
LoF obs/exp: 3 / 2.3Missense obs/exp: 72 / 84.1Syn Z: -0.30

ClinVar Variant Classifications

31 submitted variants in ClinVar

Classification Summary

Pathogenic6
Likely Pathogenic2
VUS20
6
Pathogenic
2
Likely Pathogenic
20
VUS

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
0
0
6
0
6
Likely Pathogenic
0
0
2
0
2
VUS
0
17
3
0
20
Likely Benign
0
0
0
0
0
Benign
0
0
0
0
0
Total01711028

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

LSM10 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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