LMO7DN

Chr 13

LMO7 downstream neighbor

Also known as: C13orf45, LMO7DN-IT1

LMO7DN encodes a LIM domain protein that functions in actin cytoskeleton organization and cell adhesion. Mutations cause autosomal dominant dilated cardiomyopathy with variable cardiac conduction defects and occasional skeletal muscle involvement. The gene shows very low constraint against loss-of-function variants, suggesting tolerance to protein truncation.

GOFmechanismLOEUF 1.95
Clinical SummaryLMO7DN
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.
📋
ClinVar Variants
69 unique Pathogenic / Likely Pathogenic· 7 VUS of 79 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.95LOEUF
pLI 0.000
Z-score -1.50
OE 1.66 (0.951.95)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
0.02Z-score
OE missense 0.99 (0.801.25)
54 obs / 54.3 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE1.66 (0.951.95)
00.351.4
Missense OE0.99 (0.801.25)
00.61.4
Synonymous OE0.87
01.21.6
LoF obs/exp: 10 / 6.0Missense obs/exp: 54 / 54.3Syn Z: 0.48
DN
0.5081th %ile
GOF
0.6834th %ile
LOF
0.3259th %ile

The highest-scoring mechanism for this gene is gain-of-function.

GOFprediction above median

Note: In-silico variant effect predictors (SIFT, PolyPhen, REVEL, CADD) may underestimate pathogenicity of missense variants in genes with GOF or DN mechanisms. Consider functional evidence and clinical context.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

79 submitted variants in ClinVar

Classification Summary

Pathogenic69
VUS7
Likely Benign2
69
Pathogenic
7
VUS
2
Likely Benign

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories· variant type breakdown unavailable

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
69
Likely Pathogenic
0
VUS
7
Likely Benign
2
Benign
0
Total78

Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

LMO7DN · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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