LIPT1

Chr 2AR

lipoyltransferase 1

The protein transfers lipoyl moieties to apoproteins in the second step of lipoic acid attachment to mitochondrial proteins. Mutations cause lipoyltransferase 1 deficiency, which is inherited in an autosomal recessive pattern. The pathogenic mechanism involves impaired lipoylation of mitochondrial enzyme complexes that require lipoic acid as a cofactor for proper function.

OMIMResearchSummary from RefSeq, OMIM, UniProt
ARLOEUF 1.711 OMIM phenotype
Clinical SummaryLIPT1
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Gene-Disease Validity (ClinGen)
Leigh syndrome · ARModerate

Moderate evidence — consider for supplementary testing

Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.
Some data sources returned errors (1)

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Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.71LOEUF
pLI 0.000
Z-score -0.20
OE 1.07 (0.671.71)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
0.34Z-score
OE missense 0.93 (0.821.05)
178 obs / 191.2 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE1.07 (0.671.71)
00.351.4
Missense OE0.93 (0.821.05)
00.61.4
Synonymous OE0.91
01.21.6
LoF obs/exp: 11 / 10.3Missense obs/exp: 178 / 191.2Syn Z: 0.58

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

LIPT1 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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