LDAF1

Chr 16

lipid droplet assembly factor 1

Also known as: TMEM159

The protein defines sites of lipid droplet formation in the endoplasmic reticulum in association with seipin, playing an important role in lipid and energy homeostasis. Based on current databases, no established Mendelian diseases have been definitively linked to LDAF1 mutations. The gene shows low constraint against loss-of-function variants, suggesting that complete loss may be tolerated.

OMIMResearchSummary from RefSeq, UniProt
MultiplemechanismLOEUF 1.64
Clinical SummaryLDAF1
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.64LOEUF
pLI 0.003
Z-score 0.50
OE 0.77 (0.371.64)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
0.52Z-score
OE missense 0.84 (0.701.02)
74 obs / 87.8 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.77 (0.371.64)
00.351.4
Missense OE0.84 (0.701.02)
00.61.4
Synonymous OE0.94
01.21.6
LoF obs/exp: 4 / 5.2Missense obs/exp: 74 / 87.8Syn Z: 0.28
DN
0.7326th %ile
GOF
0.79top 10%
LOF
0.3258th %ile

This gene has evidence for multiple mechanisms of pathogenicity (gain-of-function and dominant-negative). Both the Badonyi & Marsh prediction and the broader genomic evidence point to gain-of-function as the predominant mechanism. Different variants in this gene may act through different mechanisms — interpret in context of the specific variant.

GOFprediction above median
DNprediction above median

Note: In-silico variant effect predictors (SIFT, PolyPhen, REVEL, CADD) may underestimate pathogenicity of missense variants in genes with GOF or DN mechanisms. Consider functional evidence and clinical context.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

LDAF1 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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Recent Gene-Specific Literature
Gene in title · MEDLINE · newest first
Europe PMC