LAPTM4B

Chr 8

lysosomal protein transmembrane 4 beta

Also known as: LAPTM4beta, LC27

Enables ceramide binding activity; enzyme binding activity; and phosphatidylinositol bisphosphate binding activity. Involved in several processes, including endosome transport via multivesicular body sorting pathway; negative regulation of macromolecule metabolic process; and regulation of lysosomal membrane permeability. Located in several cellular components, including endosome; lysosomal membrane; and plasma membrane. [provided by Alliance of Genome Resources, Jul 2025]

0
Active trials
11
Pubs (1 yr)
0
P/LP submissions
P/LP missense
1.80
LOEUF
GOF
Mechanism· predicted
Clinical SummaryLAPTM4B
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.80LOEUF
pLI 0.000
Z-score -0.85
OE 1.25 (0.851.80)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
-0.11Z-score
OE missense 1.02 (0.911.16)
176 obs / 171.8 exp
Tolerant

Tolerant to missense variation

Observed / Expected Ratios
LoF OE1.25 (0.851.80)
00.351.4
Missense OE1.02 (0.911.16)
00.61.4
Synonymous OE1.11
01.21.6
LoF obs/exp: 17 / 13.6Missense obs/exp: 176 / 171.8Syn Z: -0.73
DN
0.5870th %ile
GOF
0.6638th %ile
LOF
0.4528th %ile

The highest-scoring mechanism for this gene is gain-of-function.

GOFprediction above median

Note: In-silico variant effect predictors (SIFT, PolyPhen, REVEL, CADD) may underestimate pathogenicity of missense variants in genes with GOF or DN mechanisms. Consider functional evidence and clinical context.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

LAPTM4B · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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Full-Text Mentions
NLP-detected gene mentions in article bodies · via PubTator3
PubTator3
Top 5 full-text resultsSearch PubTator3 ↗