KIF7

Chr 15AR

kinesin family member 7

Also known as: ACLS, AGBK, HLS2, JBTS12, MMEDF, UNQ340

This gene encodes a kinesin family protein that regulates sonic hedgehog signaling by controlling GLI transcription factors at the primary cilium, acting as both a negative regulator to prevent inappropriate GLI2 activation and a positive regulator to prevent GLI3 processing into its repressor form. Mutations cause autosomal recessive ciliopathies including Joubert syndrome 12, acrocallosal syndrome, and potentially hydrolethalus syndrome 2 and Al-Gazali-Bakalinova syndrome. The pathogenic mechanism is predicted to involve gain-of-function effects that disrupt normal hedgehog pathway regulation.

OMIMResearchSummary from RefSeq, OMIM, UniProt, Mechanism
LOFmechanismARLOEUF 0.934 OMIM phenotypes
Clinical SummaryKIF7
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.
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Clinical Trials
1 active or recruiting trial — potential therapeutic options may be available

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
0.93LOEUF
pLI 0.000
Z-score 2.02
OE 0.72 (0.560.93)
Tolerant

Typical tolerance to LoF variation

Missense Constraint
-0.69Z-score
OE missense 1.07 (1.011.13)
876 obs / 820.4 exp
Tolerant

Tolerant to missense variation

Observed / Expected Ratios
LoF OE0.72 (0.560.93)
00.351.4
Missense OE1.07 (1.011.13)
00.61.4
Synonymous OE1.07
01.21.6
LoF obs/exp: 43 / 59.9Missense obs/exp: 876 / 820.4Syn Z: -1.07
Curated Mechanism (G2P)Gene2Phenotype (DDG2P) ↗
definitiveKIF7-related acrocallosal syndromeLOFAR

Predictions shown for reference only — model trained on dominant genes, not applicable to AR conditions.

DN
0.6648th %ile
GOF
0.6638th %ile
LOF
0.3745th %ile

The Badonyi & Marsh prediction model was trained exclusively on dominant disease genes. Predictions are not reliable for genes with autosomal recessive inheritance and are shown at reduced opacity for reference only.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

KIF7 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold
Clinical Literature
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