KIF26B encodes an intracellular motor protein that transports organelles along microtubules and is essential for embryonic kidney development by maintaining mesenchymal cell adhesion adjacent to ureteric buds. Mutations cause congenital anomalies of the kidney and urinary tract (CAKUT) with autosomal recessive inheritance. The gene is highly constrained against loss-of-function variants, indicating that biallelic mutations typically result in severe developmental kidney abnormalities.

OMIMResearchSummary from RefSeq, UniProt
LOFmechanismLOEUF 0.21
Clinical SummaryKIF26B
Population Constraint (gnomAD)
Highly constrained gene — heterozygous loss-of-function variants are very rare in the population (pLI 1.00). One damaged copy is likely sufficient to cause disease.
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ClinVar Variants
36 unique Pathogenic / Likely Pathogenic· 281 VUS of 422 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

LoF intolerant — likely haploinsufficient
LoF Constraint
0.21LOEUF
pLI 1.000
Z-score 6.50
OE 0.11 (0.060.21)
Highly constrained

Highly LoF-intolerant (top ~10% of genes)

Missense Constraint
0.95Z-score
OE missense 0.92 (0.880.97)
1150 obs / 1244.0 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.11 (0.060.21)
00.351.4
Missense OE0.92 (0.880.97)
00.61.4
Synonymous OE1.09
01.21.6
LoF obs/exp: 7 / 62.3Missense obs/exp: 1150 / 1244.0Syn Z: -1.78
DN
0.4884th %ile
GOF
0.4579th %ile
LOF
0.73top 10%

The highest-scoring mechanism for this gene is loss-of-function (haploinsufficiency).

LOFprediction above median · LOEUF 0.21

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312. Mechanism ranking also informed by gnomAD constraint, ClinVar, and ClinGen data.

ClinVar Variant Classifications

422 submitted variants in ClinVar

Classification Summary

Pathogenic35
Likely Pathogenic1
VUS281
Likely Benign53
Benign25
35
Pathogenic
1
Likely Pathogenic
281
VUS
53
Likely Benign
25
Benign

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
0
0
35
0
35
Likely Pathogenic
0
0
1
0
1
VUS
0
276
5
0
281
Likely Benign
0
22
1
30
53
Benign
0
10
2
13
25
Total03084443395

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

KIF26B · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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