KCNN3

Chr 1AD

potassium calcium-activated channel subfamily N member 3

Also known as: KCa2.3, SK3, SKCA3, ZLS3, hSK3

Action potentials in vertebrate neurons are followed by an afterhyperpolarization (AHP) that may persist for several seconds and may have profound consequences for the firing pattern of the neuron. Each component of the AHP is kinetically distinct and is mediated by different calcium-activated potassium channels. This gene belongs to the KCNN family of potassium channels. It encodes an integral membrane protein that forms a voltage-independent calcium-activated channel, which is thought to regulate neuronal excitability by contributing to the slow component of synaptic AHP. This gene contains two CAG repeat regions in the coding sequence. It was thought that expansion of one or both of these repeats could lead to an increased susceptibility to schizophrenia or bipolar disorder, but studies indicate that this is probably not the case. Alternatively spliced transcript variants encoding different isoforms have been found for this gene. [provided by RefSeq, Feb 2011]

OMIMResearchGenerating clinical summary…
GOFmechanismADLOEUF 0.321 OMIM phenotype
Clinical SummaryKCNN3
Population Constraint (gnomAD)
Highly constrained gene — heterozygous loss-of-function variants are very rare in the population (pLI 0.97). One damaged copy is likely sufficient to cause disease.
📋
ClinVar Variants
7 unique Pathogenic / Likely Pathogenic· 94 VUS of 166 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Dual constrained — LoF & missense intolerant
LoF Constraint?
0.32LOEUF
pLI 0.972
Z-score 4.27
OE 0.14 (0.070.32)
Highly constrained

Highly LoF-intolerant (top ~10% of genes)

Missense Constraint?
3.33Z-score
OE missense 0.55 (0.500.62)
245 obs / 441.7 exp
Constrained

Highly missense-constrained (top ~0.1%)

Observed / Expected Ratios?
LoF OE?0.14 (0.070.32)
00.351.4
Missense OE?0.55 (0.500.62)
00.61.4
Synonymous OE?0.98
01.21.6
LoF obs/exp: 4 / 28.7Missense obs/exp: 245 / 441.7Syn Z: 0.22
Curated Mechanism (G2P)Gene2Phenotype (DDG2P) ↗
strongKCNN3-related Zimmermann-Laband syndromeGOFAD

This gene — mechanism propensity

DN
0.5869th %ile
GOF
0.7126th %ile
LOF
0.71top 10%

This gene has evidence for multiple mechanisms of pathogenicity (loss-of-function and gain-of-function). The Badonyi & Marsh model scores gain-of-function highest among its predictions, but genomic evidence (constraint, ClinVar variant spectrum, and literature) most strongly supports loss-of-function (haploinsufficiency). Different variants in this gene may act through different mechanisms — interpret in context of the specific variant.

LOFprediction above median · LOEUF 0.32
GOFprediction above median · 1 literature citation

Note: In-silico variant effect predictors (SIFT, PolyPhen, REVEL, CADD) may underestimate pathogenicity of missense variants in genes with GOF or DN mechanisms. Consider functional evidence and clinical context.

Literature Evidence

GOFGain-of-Function Mutations in KCNN3 Encoding the Small-Conductance Ca 2+-Activated K + Channel SK3 Cause Zimmermann-Laband Syndrome1

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312. Mechanism ranking also informed by gnomAD constraint, ClinVar, and ClinGen data.

References

  1. 1.PMID 31155282

ClinVar Variant Classifications

166 submitted variants in ClinVar

Classification Summary

Pathogenic4
Likely Pathogenic3
VUS94
Likely Benign36
Benign15
Conflicting4
4
Pathogenic
3
Likely Pathogenic
94
VUS
36
Likely Benign
15
Benign
4
Conflicting

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
0
4
0
0
4
Likely Pathogenic
0
2
1
0
3
VUS
8
84
2
0
94
Likely Benign
0
26
1
9
36
Benign
0
12
0
3
15
Conflicting
4
Total8128412156

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

14 pathogenic / likely-pathogenic (of 20) ClinVar copy-number / structural variants overlap KCNN3 — these span large chromosomal regions, not the gene specifically, and are excluded from the counts above. Explore in CNV tools →

Protein Context — Lollipop Plot

KCNN3 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →