KCNJ1

Chr 11AR

potassium inwardly rectifying channel subfamily J member 1

Also known as: KIR1.1, ROMK, ROMK1

Potassium channels are present in most mammalian cells, where they participate in a wide range of physiologic responses. The protein encoded by this gene is an integral membrane protein and inward-rectifier type potassium channel. It is activated by internal ATP and probably plays an important role in potassium homeostasis. The encoded protein has a greater tendency to allow potassium to flow into a cell rather than out of a cell. Mutations in this gene have been associated with antenatal Bartter syndrome, which is characterized by salt wasting, hypokalemic alkalosis, hypercalciuria, and low blood pressure. Multiple transcript variants encoding different isoforms have been found for this gene. [provided by RefSeq, Jul 2008]

GeneReviewsOMIMResearchGenerating clinical summary…

Primary Disease Associations & Inheritance

Bartter syndrome, type 2MIM #241200
AR
UniProtBartter syndrome 2, antenatal

Clinical highlights

Gene-disease validity (ClinGen)
Bartter disease type 2 · ARDefinitivesufficient evidence for diagnostic panels
0
Active trials
15
Pubs (1 yr)
P/LP submissions
P/LP missense
1.28
LOEUF
Multiple*
Mechanism· predicted
📖
GeneReview available — KCNJ1
Authoritative clinical overview · Recommended first read
Open GeneReview ↗

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint?
1.28LOEUF
pLI 0.000
Z-score 0.89
OE 0.71 (0.421.28)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint?
-0.28Z-score
OE missense 1.05 (0.941.18)
229 obs / 217.5 exp
Tolerant

Tolerant to missense variation

Observed / Expected Ratios?
LoF OE?0.71 (0.421.28)
00.351.4
Missense OE?1.05 (0.941.18)
00.61.4
Synonymous OE?0.97
01.21.6
LoF obs/exp: 8 / 11.2Missense obs/exp: 229 / 217.5Syn Z: 0.23

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

KCNJ1 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →