KCNG4

Chr 16

potassium voltage-gated channel modifier subfamily G member 4

Also known as: KV6.3, KV6.4

The KCNG4 protein functions as a regulatory subunit that modulates voltage-gated potassium channels by altering their activation, deactivation, and inactivation kinetics when coassembled with other channel subunits like KCNB1. Mutations in KCNG4 cause autosomal dominant spinocerebellar ataxia type 18, characterized by progressive cerebellar dysfunction. The gene shows autosomal dominant inheritance and has relatively low constraint to loss-of-function variation.

OMIMResearchSummary from RefSeq, UniProt
MultiplemechanismLOEUF 1.89
Clinical SummaryKCNG4
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.89LOEUF
pLI 0.000
Z-score -1.49
OE 1.43 (1.001.89)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
-1.66Z-score
OE missense 1.25 (1.161.35)
434 obs / 347.2 exp
Tolerant

Tolerant to missense variation

Observed / Expected Ratios
LoF OE1.43 (1.001.89)
00.351.4
Missense OE1.25 (1.161.35)
00.61.4
Synonymous OE1.26
01.21.6
LoF obs/exp: 20 / 14.0Missense obs/exp: 434 / 347.2Syn Z: -2.60
DN
0.73top 25%
GOF
0.86top 5%
LOF
0.2872th %ile

This gene has evidence for multiple mechanisms of pathogenicity (gain-of-function and dominant-negative). Both the Badonyi & Marsh prediction and the broader genomic evidence point to gain-of-function as the predominant mechanism. Different variants in this gene may act through different mechanisms — interpret in context of the specific variant.

GOFprediction above median
DNprediction above median

Note: In-silico variant effect predictors (SIFT, PolyPhen, REVEL, CADD) may underestimate pathogenicity of missense variants in genes with GOF or DN mechanisms. Consider functional evidence and clinical context.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

KCNG4 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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