ITPRIPL1

Chr 2

ITPRIP like 1

Also known as: D1B, KIAA1754L

The protein functions as a ligand of CD3E that inhibits T cell receptor signaling by preventing CD3E-ZAP70 interaction and downstream ERK-NFkB cascade activation. Mutations cause autosomal recessive severe combined immunodeficiency and autosomal recessive T cell immunodeficiency. The gene shows extremely low constraint against loss-of-function variants, suggesting tolerance to complete protein loss.

Summary from RefSeq, UniProt
Research Assistant →
0
Active trials
5
Pubs (1 yr)
32
P/LP submissions
0%
P/LP missense
1.37
LOEUF
Mechanism
Clinical SummaryITPRIPL1
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.
📋
ClinVar Variants
32 unique Pathogenic / Likely Pathogenic· 121 VUS of 163 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.37LOEUF
pLI 0.000
Z-score 0.39
OE 0.90 (0.611.37)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
0.53Z-score
OE missense 0.92 (0.831.01)
298 obs / 324.7 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.90 (0.611.37)
00.351.4
Missense OE0.92 (0.831.01)
00.61.4
Synonymous OE0.81
01.21.6
LoF obs/exp: 16 / 17.8Missense obs/exp: 298 / 324.7Syn Z: 1.73

ClinVar Variant Classifications

163 submitted variants in ClinVar

Classification Summary

Pathogenic22
Likely Pathogenic10
VUS121
Likely Benign4
22
Pathogenic
10
Likely Pathogenic
121
VUS
4
Likely Benign

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
0
0
22
0
22
Likely Pathogenic
0
0
10
0
10
VUS
0
88
33
0
121
Likely Benign
0
2
2
0
4
Benign
0
0
0
0
0
Total090670157

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

ITPRIPL1 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
Open Research Assistant →
Key Publications
Landmark & review papers · by relevance
PubMed
Top 3 results · since 2015Search PubMed ↗