ID1

Chr 20

inhibitor of DNA binding 1

Also known as: ID, bHLHb24

This protein functions as a transcriptional regulator that inhibits basic helix-loop-helix transcription factors by forming heterodimers and blocking their DNA binding activity, thereby regulating cellular processes including differentiation, growth, and circadian rhythms. The gene shows very low constraint against loss-of-function variants (pLI near 0, high LOEUF score), suggesting tolerance to such changes. Currently, no established Mendelian diseases have been definitively linked to ID1 mutations in clinical practice.

Summary from RefSeq, UniProt
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1
Active trials
83
Pubs (1 yr)
16
P/LP submissions
0%
P/LP missense
1.84
LOEUF
LOF
Mechanism· predicted
Clinical SummaryID1
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.
📋
ClinVar Variants
16 unique Pathogenic / Likely Pathogenic· 43 VUS of 72 total submissions
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Clinical Trials
1 active or recruiting trial — potential therapeutic options may be available

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.84LOEUF
pLI 0.000
Z-score -0.15
OE 1.07 (0.551.84)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
-2.01Z-score
OE missense 1.59 (1.391.81)
148 obs / 93.4 exp
Tolerant

Tolerant to missense variation

Observed / Expected Ratios
LoF OE1.07 (0.551.84)
00.351.4
Missense OE1.59 (1.391.81)
00.61.4
Synonymous OE1.77
01.21.6
LoF obs/exp: 5 / 4.7Missense obs/exp: 148 / 93.4Syn Z: -3.93
DN
0.4587th %ile
GOF
0.4283th %ile
LOF
0.67top 25%

The highest-scoring mechanism for this gene is loss-of-function (haploinsufficiency).

LOFprediction above median

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

72 submitted variants in ClinVar

Classification Summary

Pathogenic10
Likely Pathogenic6
VUS43
Likely Benign7
10
Pathogenic
6
Likely Pathogenic
43
VUS
7
Likely Benign

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
0
0
10
0
10
Likely Pathogenic
0
0
6
0
6
VUS
0
35
8
0
43
Likely Benign
0
0
6
1
7
Benign
0
0
0
0
0
Total03530166

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

ID1 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

Clinical Literature
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