HSPA8

Chr 11

heat shock protein family A (Hsp70) member 8

Also known as: HEL-33, HEL-S-72p, HSC54, HSC70, HSC71, HSP71, HSP73, HSPA10

The HSPA8 protein is a constitutively expressed heat shock cognate protein that functions as a molecular chaperone, facilitating protein folding, chaperone-mediated autophagy, and clathrin-coated vesicle uncoating. Mutations cause autosomal dominant neurodevelopmental disorders with intellectual disability and neurological features. This gene is highly constrained against loss-of-function variants, indicating that such mutations are likely to cause severe developmental consequences.

Summary from RefSeq, UniProt
Research Assistant →
0
Active trials
131
Pubs (1 yr)
49
P/LP submissions
0%
P/LP missense
0.20
LOEUF· LoF intol.
LOF
Mechanism· predicted
Clinical SummaryHSPA8
Population Constraint (gnomAD)
Highly constrained gene — heterozygous loss-of-function variants are very rare in the population (pLI 1.00). One damaged copy is likely sufficient to cause disease.
📋
ClinVar Variants
49 unique Pathogenic / Likely Pathogenic· 27 VUS of 104 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Dual constrained — LoF & missense intolerant
LoF Constraint
0.20LOEUF
pLI 0.999
Z-score 4.31
OE 0.04 (0.010.20)
Highly constrained

Highly LoF-intolerant (top ~10% of genes)

Missense Constraint
4.46Z-score
OE missense 0.33 (0.290.39)
119 obs / 355.7 exp
Constrained

Highly missense-constrained (top ~0.1%)

Observed / Expected Ratios
LoF OE0.04 (0.010.20)
00.351.4
Missense OE0.33 (0.290.39)
00.61.4
Synonymous OE1.82
01.21.6
LoF obs/exp: 1 / 23.6Missense obs/exp: 119 / 355.7Syn Z: -7.09
DN
0.4785th %ile
GOF
0.4184th %ile
LOF
0.71top 10%

The highest-scoring mechanism for this gene is loss-of-function (haploinsufficiency).

LOFprediction above median · LOEUF 0.20

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312. Mechanism ranking also informed by gnomAD constraint, ClinVar, and ClinGen data.

ClinVar Variant Classifications

104 submitted variants in ClinVar

Classification Summary

Pathogenic47
Likely Pathogenic2
VUS27
Likely Benign1
Benign4
47
Pathogenic
2
Likely Pathogenic
27
VUS
1
Likely Benign
4
Benign

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
0
0
47
0
47
Likely Pathogenic
0
0
2
0
2
VUS
1
23
3
0
27
Likely Benign
1
0
0
0
1
Benign
0
0
0
4
4
Total22352481

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

HSPA8 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
Open Research Assistant →