HPABH4B

Chr 14AR

GTP cyclohydrolase 1

Also known as: DYT14, DYT5, DYT5a, GCH, GTP-CH-1, GTPCH1, HPABH4B

This gene encodes GTP cyclohydrolase I, the first and rate-limiting enzyme in tetrahydrobiopterin (BH4) biosynthesis, which catalyzes the conversion of GTP into 7,8-dihydroneopterin triphosphate. BH4 serves as an essential cofactor for aromatic amino acid hydroxylases and nitric oxide synthases. Mutations cause BH4-deficient hyperphenylalaninemia, which can present as malignant hyperphenylalaninemia or dopa-responsive dystonia, and follows autosomal recessive inheritance.

Summary from RefSeq, OMIM
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Primary Disease Associations & Inheritance

Hyperphenylalaninemia, BH4-deficient, BMIM #233910
AR
0
Active trials
0
Pubs (1 yr)
0
P/LP submissions
P/LP missense
LOEUF
Mechanism
Some data sources returned errors (2)

ensembl: Error: Ensembl fetch failed: 400 for https://rest.ensembl.org/lookup/symbol/homo_sapiens/HPABH4B?content-type=application/json&expand=1

gnomad: Error: Gene not found

Population Genetics & Constraint

Constraint data not available from gnomAD.

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

HPABH4B · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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Full-Text Mentions
NLP-detected gene mentions in article bodies · via PubTator3
PubTator3
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Key Publications
Landmark & review papers · by relevance
PubMed
Top 1 results · since 2015Search PubMed ↗
Recent Gene-Specific Literature
Gene in title · MEDLINE · newest first
Europe PMC

No open access results found