HJV

Chr 1

hemojuvelin BMP co-receptor

Also known as: HFE2, HFE2A, JH, RGMC

The product of this gene is involved in iron metabolism. It may be a component of the signaling pathway which activates hepcidin or it may act as a modulator of hepcidin expression. It could also represent the cellular receptor for hepcidin. Two uORFs in the 5' UTR negatively regulate the expression and activity of the encoded protein. Alternatively spliced transcript variants encoding different isoforms have been identified for this gene. Defects in this gene are the cause of hemochromatosis type 2A, also called juvenile hemochromatosis (JH). JH is an early-onset autosomal recessive disorder due to severe iron overload resulting in hypogonadotrophic hypogonadism, hepatic fibrosis or cirrhosis and cardiomyopathy, occurring typically before age of 30. [provided by RefSeq, Oct 2015]

GeneReviewsResearchGenerating clinical summary…

Primary Disease Associations & Inheritance

UniProtHemochromatosis 2A

Clinical highlights

Gene-disease validity (ClinGen)
hemochromatosis type 2A · ARDefinitivesufficient evidence for diagnostic panels
Interpreting a novel variant
Loss of function is the curated mechanism (Gene2Phenotype), though the gene is not strongly LoF-constrained in the population — weigh truncating variants against that tolerance.Curated gene-level mechanism — a prior for triage, not a per-variant call.
0
Active trials
25
Pubs (1 yr)
P/LP submissions
P/LP missense
0.88
LOEUF
LOF
Mechanism· G2P
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GeneReview available — HJV
Authoritative clinical overview · Recommended first read
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Some data sources returned errors (1)

omim: Error: OMIM fetch failed: 429

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint?
0.88LOEUF
pLI 0.004
Z-score 1.89
OE 0.44 (0.240.88)
Tolerant

Typical tolerance to LoF variation

Missense Constraint?
-0.15Z-score
OE missense 1.03 (0.931.14)
247 obs / 240.3 exp
Tolerant

Tolerant to missense variation

Observed / Expected Ratios?
LoF OE?0.44 (0.240.88)
00.351.4
Missense OE?1.03 (0.931.14)
00.61.4
Synonymous OE?0.94
01.21.6
LoF obs/exp: 6 / 13.5Missense obs/exp: 247 / 240.3Syn Z: 0.43

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

HJV · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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