HELLS

Chr 10AR

helicase, lymphoid specific

Also known as: ICF4, LSH, Nbla10143, PASG, SALNR, SMARCA6

This gene encodes an ATP-dependent chromatin remodeler that regulates chromatin accessibility, DNA methylation, and histone modifications, and is involved in DNA repair and genomic stability. Mutations cause immunodeficiency-centromeric instability-facial anomalies syndrome 4, inherited in an autosomal recessive pattern. The gene is highly constrained against loss-of-function variants (pLI = 1.00, LOEUF = 0.24), indicating that complete loss of protein function is poorly tolerated.

OMIMResearchSummary from RefSeq, OMIM, UniProt
ARLOEUF 0.241 OMIM phenotype
Clinical SummaryHELLS
🧬
Gene-Disease Validity (ClinGen)
immunodeficiency-centromeric instability-facial anomalies syndrome 4 · ARModerate

Moderate evidence — consider for supplementary testing

Population Constraint (gnomAD)
Highly constrained gene — heterozygous loss-of-function variants are very rare in the population (pLI 1.00). One damaged copy is likely sufficient to cause disease.
📋
ClinVar Variants
31 unique Pathogenic / Likely Pathogenic· 169 VUS of 499 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

LoF intolerant — likely haploinsufficient
LoF Constraint
0.24LOEUF
pLI 1.000
Z-score 6.01
OE 0.13 (0.070.24)
Highly constrained

Highly LoF-intolerant (top ~10% of genes)

Missense Constraint
2.99Z-score
OE missense 0.60 (0.540.66)
258 obs / 433.3 exp
Mild constraint

Moderately missense-constrained (top ~2.5%)

Observed / Expected Ratios
LoF OE0.13 (0.070.24)
00.351.4
Missense OE0.60 (0.540.66)
00.61.4
Synonymous OE1.02
01.21.6
LoF obs/exp: 7 / 55.1Missense obs/exp: 258 / 433.3Syn Z: -0.15

ClinVar Variant Classifications

499 submitted variants in ClinVar

Classification Summary

Pathogenic26
Likely Pathogenic5
VUS169
Likely Benign261
Benign21
Conflicting4
26
Pathogenic
5
Likely Pathogenic
169
VUS
261
Likely Benign
21
Benign
4
Conflicting

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
10
0
16
0
26
Likely Pathogenic
4
0
1
0
5
VUS
1
150
17
1
169
Likely Benign
0
7
131
123
261
Benign
0
0
15
6
21
Conflicting
4
Total15157180130486

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

HELLS · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
Open Research Assistant →
Full-Text Mentions
NLP-detected gene mentions in article bodies · via PubTator3
PubTator3
Development hell.
Kinney BC·Nature
2023
From hell to paradise.
Villalobos Santos J·Emergencias
2023
Travelling to hell and back
Polastri M·Intensive Care Med
2021
What version of Hell's Kitchen?
Peck TE et al.·Anaesthesia
2022
Top 5 full-text resultsSearch PubTator3 ↗