H1-0

Chr 22

H1.0 linker histone

Also known as: H1.0, H10, H1F0, H1FV

The H1-0 protein binds to linker DNA between nucleosomes to form higher-order chromatin structures and is particularly expressed in terminally differentiated cells with low division rates. Mutations in H1-0 cause neurodevelopmental disorder with spastic diplegia and visual defects, which follows an autosomal dominant inheritance pattern. This condition typically presents in early childhood with developmental delays affecting motor and visual systems.

OMIMResearchSummary from RefSeq, UniProt
LOFmechanismLOEUF 0.90
Clinical SummaryH1-0
Population Constraint (gnomAD)
Moderately constrained gene (pLI 0.64) — some intolerance to loss-of-function variants.
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Clinical Trials
12 active or recruiting trials — potential therapeutic options may be available

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Moderate LoF intolerance
LoF Constraint
0.90LOEUF
pLI 0.643
Z-score 1.69
OE 0.00 (0.000.90)
Moderately constrained

Typical tolerance to LoF variation

Missense Constraint
0.88Z-score
OE missense 0.77 (0.650.92)
88 obs / 114.4 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.00 (0.000.90)
00.351.4
Missense OE0.77 (0.650.92)
00.61.4
Synonymous OE1.23
01.21.6
LoF obs/exp: 0 / 3.3Missense obs/exp: 88 / 114.4Syn Z: -1.32
DN
0.4289th %ile
GOF
0.12100th %ile
LOF
0.69top 10%

The highest-scoring mechanism for this gene is loss-of-function (haploinsufficiency).

LOFprediction above median

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

H1-0 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

Fatigue

The Role of the Brain in Mental and Physical Fatigue

RECRUITING
NCT05880342Phase PHASE3Vrije Universiteit BrusselStarted 2023-05-03
Reboxetine PillMethylphenidate Oral Product
DyslipidemiaCardiopulmonary Fitness

Effects of a 12-Week Waltz Dance Intervention on Cardiovascular Health in Women Aged 45-65 With Dyslipidemia

NOT YET RECRUITING
NCT07061249Phase NAGdansk University of Physical Education and SportStarted 2025-07-05
Waltz Dance
Aggression

Virtual Reality Intervention (VR-GINSO) for Reducing Aggression in Young Offenders

RECRUITING
NCT07484919Phase NAUniversidad Francisco de VitoriaStarted 2025-12-15
Virtual RealityActive ControlTreatment as usual
Multiple Sclerosis

Noninvasive Vagal Nerve Stimulation

RECRUITING
NCT06816004Phase NANYU Langone HealthStarted 2025-08-20
Remotely Supervised Transcranial Direct Current Stimulation (RS - tDCS)Remotely Supervised Transcutaneous Auricular Vagus Nerve Stimulation (RS - taVNS)Remotely Supervised Transcutaneous Cervical Vagus Nerve Stimulation (RS - tcVNS)
Aging

Aquatic Exercises Combined With Cognitive Tasks for Older Adults

RECRUITING
NCT07156708Phase NAFederal University of PelotasStarted 2025-09-05
Aquatic aerobic exercise programCognitive tasks
Anterior Shoulder Dislocation

Apprehension-based Training Compared With Standard Physical Therapy for Military Personnel Following Anterior Shoulder Dislocation - a Randomized Clinical Trial

RECRUITING
NCT06752551Phase NAAlon RabinStarted 2025-02-05
Apprehension-based trainingStandard physical therapy
Healthy Adult Male and Female Volunteers

Diaphragmatic Breathing and Stimulation of the Autonomic Nervous System

NOT YET RECRUITING
NCT07445113Phase NAUniversity of JaénStarted 2026-02-15
Guided breathing at 6 breaths per minute (bpm) with an inspiration (I) to expiration (E)Guided breathing at 6 bpm with apnea (A)Breathing education
Anxiety

The Effectiveness of Press Needle Acupuncture on Preoperative Anxiety in Tympanoplasty and Mastoidectomy

RECRUITING
NCT07278284Phase NAIndonesia UniversityStarted 2026-01-18
The press needle acupunctureThe sham press needle acupuncture
Triple-Negative Breast Cancer (TNBC)

Metabolic Flexibility in Patients With Early Triple-negative Breast Cancer

ACTIVE NOT RECRUITING
NCT07484776Phase NAUniversidad Europea de MadridStarted 2026-02-10
Cardiovascular training at maximal fat oxidation (FATmax)Cardiovascular training at maximal aerobic power (MAP)Resistance training
Eating Disorders

Targeting Transdiagnostic Self-regulatory Factors and Eating Disorder Pathology Among Adults With BInge-spectrum Eating disOrders: A mHEALTH Interoceptive Exposure Intervention (the Bio-HEALTH Study)

RECRUITING
NCT06631729Phase NAUniversity of MinnesotaStarted 2025-01-15
HRV-bioED-JITAI
Transient; Hypoglycemia, NeonatalPretermGlibenclamide Adverse Reaction

Oral Glibenclamide in Preterm Infants With Hyperglycaemia (GALOP)

ACTIVE NOT RECRUITING
NCT05687500Phase PHASE2Assistance Publique - Hôpitaux de ParisStarted 2023-05-20
GlibenclamidePharmacokinetics studyC-peptide proinsulin ratio
Vagus Nerve StimulationAutonomic Nervous SystemHeart Rate

Frequency-Dependent Effects of Auricular Vagus Nerve Stimulation on Autonomic and Cardiovascular Parameters

NOT YET RECRUITING
NCT07274332Phase NASEFA HAKTAN HATIKStarted 2025-12-22
Pulsetto FIT™ - Sham tcVNSPulsetto FIT™ - tcVNS 10 HzPulsetto FIT™ - tcVNS 25 Hz
Clinical Literature
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