GPRASP3

Chr X

G protein-coupled receptor associated sorting protein family member 3

Also known as: BHLHB9, GASP3, p60TRP

The encoded protein promotes neuronal survival and differentiation and regulates neurosynaptogenesis by inducing phosphatase PP2A activity, which leads to APP dephosphorylation and inhibits BACE1-mediated APP processing. Mutations in GPRASP3 cause autosomal recessive neurodevelopmental disorders affecting the central nervous system. The gene shows relatively low constraint to loss-of-function variation.

Summary from RefSeq, UniProt
Research Assistant →
0
Active trials
0
Pubs (1 yr)
0
P/LP submissions
P/LP missense
1.02
LOEUF
GOF
Mechanism· predicted
Clinical SummaryGPRASP3
Population Constraint (gnomAD)
Low constraint (pLI 0.02) — loss-of-function variants are relatively tolerated in the population.

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.02LOEUF
pLI 0.020
Z-score 1.55
OE 0.44 (0.221.02)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
0.47Z-score
OE missense 0.91 (0.801.02)
180 obs / 198.8 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.44 (0.221.02)
00.351.4
Missense OE0.91 (0.801.02)
00.61.4
Synonymous OE0.70
01.21.6
LoF obs/exp: 4 / 9.0Missense obs/exp: 180 / 198.8Syn Z: 1.97
DN
0.5673th %ile
GOF
0.74top 25%
LOF
0.3746th %ile

The highest-scoring mechanism for this gene is gain-of-function.

GOFprediction above median

Note: In-silico variant effect predictors (SIFT, PolyPhen, REVEL, CADD) may underestimate pathogenicity of missense variants in genes with GOF or DN mechanisms. Consider functional evidence and clinical context.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

GPRASP3 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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Full-Text Mentions
NLP-detected gene mentions in article bodies · via PubTator3
PubTator3
Top 3 full-text resultsSearch PubTator3 ↗
Key Publications
Landmark & review papers · by relevance
PubMed
Top 2 results · since 2015Search PubMed ↗
Recent Gene-Specific Literature
Gene in title · MEDLINE · newest first
Europe PMC

No open access results found