GLRA1

Chr 5

glycine receptor alpha 1

Also known as: HKPX1, STHE

The protein encoded by this gene is a subunit of a pentameric inhibitory glycine receptor, which mediates postsynaptic inhibition in the central nervous system. Defects in this gene are a cause of startle disease (STHE), also known as hereditary hyperekplexia or congenital stiff-person syndrome. Multiple transcript variants encoding different isoforms have been found. [provided by RefSeq, Dec 2015]

GeneReviewsResearchGenerating clinical summary…

Primary Disease Associations & Inheritance

UniProtHyperekplexia 1

Clinical highlights

Interpreting a novel variant
Loss of function is the curated mechanism (Gene2Phenotype), though the gene is not strongly LoF-constrained in the population — weigh truncating variants against that tolerance.Curated gene-level mechanism — a prior for triage, not a per-variant call.
3
Active trials
11
Pubs (1 yr)
P/LP submissions
P/LP missense
0.76
LOEUF
LOF*
Mechanism· G2P
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GeneReview available — GLRA1
Authoritative clinical overview · Recommended first read
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Some data sources returned errors (1)

omim: Error: OMIM fetch failed: 429

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint?
0.76LOEUF
pLI 0.000
Z-score 2.41
OE 0.45 (0.280.76)
Tolerant

Typical tolerance to LoF variation

Missense Constraint?
1.42Z-score
OE missense 0.75 (0.670.85)
195 obs / 259.4 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios?
LoF OE?0.45 (0.280.76)
00.351.4
Missense OE?0.75 (0.670.85)
00.61.4
Synonymous OE?1.00
01.21.6
LoF obs/exp: 10 / 22.3Missense obs/exp: 195 / 259.4Syn Z: 0.02

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

GLRA1 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.