GLIPR2

Chr 9

GLI pathogenesis related 2

Also known as: C9orf19, GAPR-1, GAPR1, gliPR 2

The protein enables homodimerization and is involved in positive regulation of ERK1/ERK2 signaling cascade, epithelial cell migration, and epithelial to mesenchymal transition, and is located in the Golgi membrane. Mutations cause autosomal recessive neurodevelopmental disorder with epilepsy and brain atrophy. The gene is not highly constrained against loss-of-function variants.

OMIMResearchSummary from RefSeq
DNmechanismLOEUF 1.59
Clinical SummaryGLIPR2
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.59LOEUF
pLI 0.000
Z-score 0.34
OE 0.87 (0.491.59)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
0.31Z-score
OE missense 0.91 (0.771.09)
87 obs / 95.4 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.87 (0.491.59)
00.351.4
Missense OE0.91 (0.771.09)
00.61.4
Synonymous OE1.01
01.21.6
LoF obs/exp: 7 / 8.1Missense obs/exp: 87 / 95.4Syn Z: -0.07
DN
0.6744th %ile
GOF
0.5758th %ile
LOF
0.2580th %ile

The highest-scoring mechanism for this gene is dominant-negative.

DNprediction above median

Note: In-silico variant effect predictors (SIFT, PolyPhen, REVEL, CADD) may underestimate pathogenicity of missense variants in genes with GOF or DN mechanisms. Consider functional evidence and clinical context.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

GLIPR2 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
Open Research Assistant →
Key Publications
Landmark & review papers · by relevance
PubMed
Top 1 results · since 2015Search PubMed ↗