GFRA2

Chr 8

GDNF family receptor alpha 2

Also known as: GDNFRB, NRTNR-ALPHA, NTNRA, RETL2, TRNR2

The protein is a GPI-linked cell surface receptor that binds neurturin and GDNF to activate the RET tyrosine kinase receptor, supporting survival of sympathetic neurons. GFRA2 mutations cause congenital central hypoventilation syndrome and Hirschsprung disease through autosomal dominant inheritance. The gene shows moderate constraint against loss-of-function variants (LOEUF 0.69), and these conditions affect the autonomic nervous system with onset in the neonatal period.

Summary from RefSeq, UniProt
Research Assistant →
0
Active trials
7
Pubs (1 yr)
80
P/LP submissions
0%
P/LP missense
0.69
LOEUF
Mechanism
Clinical SummaryGFRA2
Population Constraint (gnomAD)
Constrained for loss-of-function variants (OE-LoF 0.30) despite low pLI — interpret in context.
📋
ClinVar Variants
80 unique Pathogenic / Likely Pathogenic· 69 VUS of 161 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
0.69LOEUF
pLI 0.098
Z-score 2.36
OE 0.30 (0.150.69)
Tolerant

Typical tolerance to LoF variation

Missense Constraint
0.14Z-score
OE missense 0.97 (0.861.10)
191 obs / 196.6 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.30 (0.150.69)
00.351.4
Missense OE0.97 (0.861.10)
00.61.4
Synonymous OE1.20
01.21.6
LoF obs/exp: 4 / 13.3Missense obs/exp: 191 / 196.6Syn Z: -1.44

ClinVar Variant Classifications

161 submitted variants in ClinVar

Classification Summary

Pathogenic77
Likely Pathogenic3
VUS69
Likely Benign2
Benign2
77
Pathogenic
3
Likely Pathogenic
69
VUS
2
Likely Benign
2
Benign

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
0
0
77
0
77
Likely Pathogenic
0
0
3
0
3
VUS
0
61
8
0
69
Likely Benign
0
1
1
0
2
Benign
0
1
0
1
2
Total063891153

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

GFRA2 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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