GALE

Chr 1AR

UDP-galactose-4-epimerase

Also known as: SDR1E1, THC13

The encoded UDP-galactose-4-epimerase catalyzes the epimerization of UDP-glucose to UDP-galactose and UDP-N-acetylglucosamine to UDP-N-acetylgalactosamine, making cells dependent on both exogenous galactose and N-acetylgalactosamine for glycoprotein and glycolipid synthesis. Mutations cause autosomal recessive epimerase-deficiency galactosemia (galactosemia type 3), characterized by liver damage, early-onset cataracts, deafness, and cognitive disability with variable severity from mild peripheral to severe generalized forms. Mutations also cause thrombocytopenia 13, syndromic.

OMIMResearchSummary from RefSeq, OMIM, Mechanism
LOFmechanismARLOEUF 1.392 OMIM phenotypes
Clinical SummaryGALE
🧬
Gene-Disease Validity (ClinGen)
galactose epimerase deficiency · ARDefinitive

Definitive — sufficient evidence for diagnostic panels

Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.
💊
Clinical Trials
1 active or recruiting trial — potential therapeutic options may be available

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.39LOEUF
pLI 0.000
Z-score 0.33
OE 0.91 (0.621.39)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
-0.32Z-score
OE missense 1.06 (0.951.19)
217 obs / 204.0 exp
Tolerant

Tolerant to missense variation

Observed / Expected Ratios
LoF OE0.91 (0.621.39)
00.351.4
Missense OE1.06 (0.951.19)
00.61.4
Synonymous OE1.00
01.21.6
LoF obs/exp: 16 / 17.5Missense obs/exp: 217 / 204.0Syn Z: 0.01
Curated Mechanism (G2P)Gene2Phenotype (DDG2P) ↗
definitiveGALE-related epimerase-deficiency galactosemiaLOFAR

Predictions shown for reference only — model trained on dominant genes, not applicable to AR conditions.

DN
0.6936th %ile
GOF
0.4677th %ile
LOF
0.3842th %ile

The Badonyi & Marsh prediction model was trained exclusively on dominant disease genes. Predictions are not reliable for genes with autosomal recessive inheritance and are shown at reduced opacity for reference only.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

GALE · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold
Clinical Literature
Open Research Assistant →
Full-Text Mentions
NLP-detected gene mentions in article bodies · via PubTator3
PubTator3
Top 5 full-text resultsSearch PubTator3 ↗