G6PD

Chr XX-linked

glucose-6-phosphate dehydrogenase

Also known as: CNSHA1, G6PD1

Glucose-6-phosphate dehydrogenase catalyzes the rate-limiting step of the oxidative pentose-phosphate pathway, producing NADPH which provides crucial reducing power for cellular defense against oxidizing agents and for biosynthetic reactions. Mutations cause G6PD deficiency, resulting in congenital nonspherocytic hemolytic anemia with variable severity ranging from neonatal jaundice to acute hemolytic episodes or severe chronic anemia. The gene shows X-linked inheritance and is highly constrained against loss-of-function variants, with numerous missense variants described that produce wide-ranging levels of enzyme activity.

GeneReviewsOMIMResearchSummary from RefSeq, OMIM, UniProt
X-linkedLOEUF 0.322 OMIM phenotypes
Clinical SummaryG6PD
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Gene-Disease Validity (ClinGen)
G6PD deficiency · XLDefinitive

Definitive — sufficient evidence for diagnostic panels

2 total gene-disease associations curated

Population Constraint (gnomAD)
Highly constrained gene — heterozygous loss-of-function variants are very rare in the population (pLI 0.97). One damaged copy is likely sufficient to cause disease.
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Clinical Trials
1 active or recruiting trial — potential therapeutic options may be available
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GeneReview available — G6PD
Authoritative clinical overview · Recommended first read
Open GeneReview ↗

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

LoF intolerant — likely haploinsufficient
LoF Constraint
0.32LOEUF
pLI 0.972
Z-score 3.71
OE 0.10 (0.040.32)
Highly constrained

Highly LoF-intolerant (top ~10% of genes)

Missense Constraint
2.00Z-score
OE missense 0.65 (0.580.74)
174 obs / 265.8 exp
Mild constraint

Moderately missense-constrained (top ~2.5%)

Observed / Expected Ratios
LoF OE0.10 (0.040.32)
00.351.4
Missense OE0.65 (0.580.74)
00.61.4
Synonymous OE1.00
01.21.6
LoF obs/exp: 2 / 19.8Missense obs/exp: 174 / 265.8Syn Z: -0.03

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

G6PD · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold
Clinical Literature
Open Research Assistant →
Full-Text Mentions
NLP-detected gene mentions in article bodies · via PubTator3
PubTator3
Top 5 full-text resultsSearch PubTator3 ↗
Key Publications
Landmark & review papers · by relevance
PubMed
Top 5 results · since 2015Search PubMed ↗