FURIN

Chr 15

furin, paired basic amino acid cleaving enzyme

Also known as: FUR, PACE, PCSK3, SPC1

The FURIN protein is an endoprotease that cleaves protein precursors at specific basic amino acid sequences within the secretory pathway, processing substrates including growth factors, hormones, and other signaling molecules. Pathogenic variants cause autosomal dominant developmental delay with variable intellectual disability, behavioral abnormalities, and distinctive facial features. This gene is highly constrained against loss-of-function variants, reflecting its essential role in cellular protein processing.

GeneReviewsOMIMResearchSummary from RefSeq, UniProt
LOEUF 0.19
Clinical SummaryFURIN
Population Constraint (gnomAD)
Highly constrained gene — heterozygous loss-of-function variants are very rare in the population (pLI 1.00). One damaged copy is likely sufficient to cause disease.
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Clinical Trials
1 active or recruiting trial — potential therapeutic options may be available
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GeneReview available — FURIN
Authoritative clinical overview · Recommended first read
Open GeneReview ↗

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

LoF intolerant — likely haploinsufficient
LoF Constraint
0.19LOEUF
pLI 1.000
Z-score 5.47
OE 0.07 (0.030.19)
Highly constrained

Highly LoF-intolerant (top ~10% of genes)

Missense Constraint
2.50Z-score
OE missense 0.69 (0.640.76)
366 obs / 527.8 exp
Mild constraint

Moderately missense-constrained (top ~2.5%)

Observed / Expected Ratios
LoF OE0.07 (0.030.19)
00.351.4
Missense OE0.69 (0.640.76)
00.61.4
Synonymous OE1.05
01.21.6
LoF obs/exp: 3 / 40.7Missense obs/exp: 366 / 527.8Syn Z: -0.66

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

FURIN · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold
Clinical Literature
Open Research Assistant →
Full-Text Mentions
NLP-detected gene mentions in article bodies · via PubTator3
PubTator3
Top 5 full-text resultsSearch PubTator3 ↗
Key Publications
Landmark & review papers · by relevance
PubMed
Top 5 results · since 2015Search PubMed ↗