This protein functions as a transcriptional activator that regulates MEF2C and plays important roles in skeletal muscle fiber identity, muscle regeneration, and spermatogenesis. Mutations cause autosomal dominant neurodevelopmental disorders with intellectual disability, developmental delays, and various congenital anomalies. The gene is highly constrained against loss-of-function mutations, indicating intolerance to protein-disrupting variants.

OMIMResearchSummary from RefSeq, UniProt
LOFmechanismLOEUF 0.27
Clinical SummaryFOXJ3
Population Constraint (gnomAD)
Highly constrained gene — heterozygous loss-of-function variants are very rare in the population (pLI 1.00). One damaged copy is likely sufficient to cause disease.

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

LoF intolerant — likely haploinsufficient
LoF Constraint
0.27LOEUF
pLI 0.996
Z-score 4.76
OE 0.12 (0.060.27)
Highly constrained

Highly LoF-intolerant (top ~10% of genes)

Missense Constraint
1.31Z-score
OE missense 0.80 (0.720.88)
271 obs / 339.0 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.12 (0.060.27)
00.351.4
Missense OE0.80 (0.720.88)
00.61.4
Synonymous OE1.12
01.21.6
LoF obs/exp: 4 / 33.9Missense obs/exp: 271 / 339.0Syn Z: -1.02
DN
0.2997th %ile
GOF
0.2895th %ile
LOF
0.83top 5%

The highest-scoring mechanism for this gene is loss-of-function (haploinsufficiency).

LOFprediction above median · LOEUF 0.27

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312. Mechanism ranking also informed by gnomAD constraint, ClinVar, and ClinGen data.

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

FOXJ3 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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Full-Text Mentions
NLP-detected gene mentions in article bodies · via PubTator3
PubTator3
Top 5 full-text resultsSearch PubTator3 ↗