FEM1C

Chr 5

fem-1 homolog C

Also known as: EUROIMAGE686608, EUROIMAGE783647, FEM1A

The protein serves as a substrate-recognition component of a Cul2-RING E3 ubiquitin ligase complex that targets proteins with specific C-terminal degrons for ubiquitination and degradation. Mutations in FEM1C cause autosomal recessive intellectual disability with seizures and hypotonia. This gene shows significant constraint against loss-of-function variants (LOEUF 0.479), suggesting that complete protein loss is likely pathogenic.

OMIMResearchSummary from RefSeq, UniProt
DNmechanismLOEUF 0.48
Clinical SummaryFEM1C
Population Constraint (gnomAD)
Moderately constrained gene (pLI 0.63) — some intolerance to loss-of-function variants.

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Moderate LoF intolerance
LoF Constraint
0.48LOEUF
pLI 0.629
Z-score 3.04
OE 0.19 (0.080.48)
Moderately constrained

More LoF-intolerant than ~75% of genes

Missense Constraint
2.43Z-score
OE missense 0.63 (0.560.70)
212 obs / 337.7 exp
Mild constraint

Moderately missense-constrained (top ~2.5%)

Observed / Expected Ratios
LoF OE0.19 (0.080.48)
00.351.4
Missense OE0.63 (0.560.70)
00.61.4
Synonymous OE0.95
01.21.6
LoF obs/exp: 3 / 16.2Missense obs/exp: 212 / 337.7Syn Z: 0.40

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

FEM1C · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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Recent Gene-Specific Literature
Gene in title · MEDLINE · newest first
Europe PMC