FAM90A1

Chr 12

family with sequence similarity 90 member A1

The FAM90A1 protein belongs to a primate-specific gene family that arose from multiple duplications and rearrangements, though its specific molecular function remains unclear. This gene is highly constrained against loss-of-function variants, but no human diseases have been definitively associated with FAM90A1 mutations to date.

Summary from RefSeq
Research Assistant →
0
Active trials
2
Pubs (1 yr)
39
P/LP submissions
0%
P/LP missense
1.87
LOEUF
DN
Mechanism· predicted
Clinical SummaryFAM90A1
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.
📋
ClinVar Variants
38 unique Pathogenic / Likely Pathogenic· 95 VUS of 159 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.87LOEUF
pLI 0.000
Z-score -0.56
OE 1.24 (0.711.87)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
-1.43Z-score
OE missense 1.25 (1.141.37)
328 obs / 262.7 exp
Tolerant

Tolerant to missense variation

Observed / Expected Ratios
LoF OE1.24 (0.711.87)
00.351.4
Missense OE1.25 (1.141.37)
00.61.4
Synonymous OE1.42
01.21.6
LoF obs/exp: 8 / 6.5Missense obs/exp: 328 / 262.7Syn Z: -3.47
DN
0.6452th %ile
GOF
0.5071th %ile
LOF
0.4134th %ile

The highest-scoring mechanism for this gene is dominant-negative.

DNprediction above median

Note: In-silico variant effect predictors (SIFT, PolyPhen, REVEL, CADD) may underestimate pathogenicity of missense variants in genes with GOF or DN mechanisms. Consider functional evidence and clinical context.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

159 submitted variants in ClinVar

Classification Summary

Pathogenic36
Likely Pathogenic2
VUS95
Likely Benign10
Benign8
36
Pathogenic
2
Likely Pathogenic
95
VUS
10
Likely Benign
8
Benign

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
0
0
36
0
36
Likely Pathogenic
0
0
2
0
2
VUS
0
91
4
0
95
Likely Benign
0
6
2
2
10
Benign
0
3
5
0
8
Total0100492151

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

FAM90A1 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
Open Research Assistant →
Full-Text Mentions
NLP-detected gene mentions in article bodies · via PubTator3
PubTator3
Top 5 full-text resultsSearch PubTator3 ↗
Key Publications
Landmark & review papers · by relevance
PubMed
Top 2 results · since 2015Search PubMed ↗
Recent Gene-Specific Literature
Gene in title · MEDLINE · newest first
Europe PMC

No open access results found