FAM234B

Chr 12

family with sequence similarity 234 member B

Also known as: KIAA1467

The FAM234B protein is predicted to localize to the Golgi apparatus, membrane, and microtubule organizing center, though its specific molecular function remains unclear. Mutations in this gene cause autosomal recessive developmental delay with seizures and microcephaly, representing a rare neurodevelopmental disorder with onset in early childhood. The gene shows moderate constraint against loss-of-function variants (LOEUF 0.499), consistent with its role in normal neurodevelopment.

Summary from RefSeq
Research Assistant →
0
Active trials
1
Pubs (1 yr)
45
P/LP submissions
0%
P/LP missense
0.50
LOEUF
Mechanism
Clinical SummaryFAM234B
Population Constraint (gnomAD)
Constrained for loss-of-function variants (OE-LoF 0.29) despite low pLI — interpret in context.
📋
ClinVar Variants
45 unique Pathogenic / Likely Pathogenic· 75 VUS of 151 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Moderate LoF intolerance
LoF Constraint
0.50LOEUF
pLI 0.025
Z-score 3.71
OE 0.29 (0.170.50)
Moderately constrained

More LoF-intolerant than ~75% of genes

Missense Constraint
0.49Z-score
OE missense 0.93 (0.851.01)
329 obs / 355.0 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.29 (0.170.50)
00.351.4
Missense OE0.93 (0.851.01)
00.61.4
Synonymous OE1.15
01.21.6
LoF obs/exp: 9 / 31.5Missense obs/exp: 329 / 355.0Syn Z: -1.42

ClinVar Variant Classifications

151 submitted variants in ClinVar

Classification Summary

Pathogenic43
Likely Pathogenic2
VUS75
Likely Benign13
Benign6
43
Pathogenic
2
Likely Pathogenic
75
VUS
13
Likely Benign
6
Benign

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
0
0
43
0
43
Likely Pathogenic
0
0
2
0
2
VUS
0
70
5
0
75
Likely Benign
0
6
0
7
13
Benign
0
3
0
3
6
Total0795010139

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

FAM234B · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
Open Research Assistant →
Key Publications
Landmark & review papers · by relevance
PubMed
Top 1 results · since 2015Search PubMed ↗
Recent Gene-Specific Literature
Gene in title · MEDLINE · newest first
Europe PMC