ESS2

Chr 22

ess-2 splicing factor homolog

The ESS2 protein is involved in pre-mRNA splicing and may function as a component of C complex spliceosomes. Mutations cause developmental disorders including DiGeorge syndrome, velocardiofacial syndrome, and conotruncal anomaly face syndrome, typically arising from 22q11.2 microdeletions that encompass this gene along with others in the minimal DiGeorge critical region. These disorders follow an autosomal dominant inheritance pattern and primarily affect cardiac, craniofacial, and immune system development.

OMIMResearchSummary from RefSeq, UniProt
DNmechanismLOEUF 0.96
Clinical SummaryESS2
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.
Some data sources returned errors (1)

ncbi: Error: NCBI fetch failed: 429 https://eutils.ncbi.nlm.nih.gov/entrez/eutils/esearch.fcgi

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
0.96LOEUF
pLI 0.000
Z-score 1.71
OE 0.61 (0.400.96)
Tolerant

Typical tolerance to LoF variation

Missense Constraint
0.27Z-score
OE missense 0.96 (0.861.06)
273 obs / 285.8 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.61 (0.400.96)
00.351.4
Missense OE0.96 (0.861.06)
00.61.4
Synonymous OE1.22
01.21.6
LoF obs/exp: 14 / 22.8Missense obs/exp: 273 / 285.8Syn Z: -1.89
DN
0.7131th %ile
GOF
0.5465th %ile
LOF
0.4529th %ile

The highest-scoring mechanism for this gene is dominant-negative.

DNprediction above median

Note: In-silico variant effect predictors (SIFT, PolyPhen, REVEL, CADD) may underestimate pathogenicity of missense variants in genes with GOF or DN mechanisms. Consider functional evidence and clinical context.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

ESS2 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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