ERN2

Chr 16

endoplasmic reticulum to nucleus signaling 2

Also known as: IRE1-BETA, IRE1b, IRE2p, hIRE2p

The ERN2 protein is a kinase that cleaves 28S ribosomal RNA to induce translational repression during endoplasmic reticulum stress and promotes apoptosis. Mutations cause autosomal recessive developmental and epileptic encephalopathy with microcephaly, typically presenting in early infancy with severe developmental delay, refractory seizures, and progressive microcephaly. This gene is not highly constrained against loss-of-function variants in the general population.

OMIMResearchSummary from RefSeq, UniProt
LOEUF 1.03
Clinical SummaryERN2
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.03LOEUF
pLI 0.000
Z-score 1.38
OE 0.80 (0.621.03)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
-0.29Z-score
OE missense 1.03 (0.971.11)
587 obs / 567.2 exp
Tolerant

Tolerant to missense variation

Observed / Expected Ratios
LoF OE0.80 (0.621.03)
00.351.4
Missense OE1.03 (0.971.11)
00.61.4
Synonymous OE0.99
01.21.6
LoF obs/exp: 42 / 52.8Missense obs/exp: 587 / 567.2Syn Z: 0.08

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

ERN2 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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Recent Gene-Specific Literature
Gene in title · MEDLINE · newest first
Europe PMC