ERICH1

Chr 8

glutamate rich 1

Also known as: HSPC319

The protein localizes to the endoplasmic reticulum and functions as a transmembrane protein involved in cellular processes, though its specific molecular role remains incompletely characterized. Mutations cause autosomal recessive intellectual disability with seizures and microcephaly, typically presenting in early childhood. The gene shows tolerance to loss-of-function variants (very low pLI score), consistent with the recessive inheritance pattern observed in affected families.

0
Active trials
0
Pubs (1 yr)
129
P/LP submissions
0%
P/LP missense
1.64
LOEUF
Mechanism
Clinical SummaryERICH1
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.
📋
ClinVar Variants
128 unique Pathogenic / Likely Pathogenic· 134 VUS of 291 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.64LOEUF
pLI 0.000
Z-score -0.53
OE 1.14 (0.801.64)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
-2.66Z-score
OE missense 1.46 (1.341.59)
388 obs / 266.0 exp
Tolerant

Tolerant to missense variation

Observed / Expected Ratios
LoF OE1.14 (0.801.64)
00.351.4
Missense OE1.46 (1.341.59)
00.61.4
Synonymous OE1.43
01.21.6
LoF obs/exp: 20 / 17.6Missense obs/exp: 388 / 266.0Syn Z: -3.57

ClinVar Variant Classifications

291 submitted variants in ClinVar

Classification Summary

Pathogenic121
Likely Pathogenic7
VUS134
Likely Benign14
121
Pathogenic
7
Likely Pathogenic
134
VUS
14
Likely Benign

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
0
0
121
0
121
Likely Pathogenic
0
0
7
0
7
VUS
0
108
26
0
134
Likely Benign
0
7
7
0
14
Benign
0
0
0
0
0
Total01151610276

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

ERICH1 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
Open Research Assistant →
Key Publications
Landmark & review papers · by relevance
PubMed
Top 1 results · since 2015Search PubMed ↗
Recent Gene-Specific Literature
Gene in title · MEDLINE · newest first
Europe PMC

No open access results found