ENTPD3

Chr 3

ectonucleoside triphosphate diphosphohydrolase 3

Also known as: CD39L3, HB6, NTPDase-3

This gene encodes a plasma membrane nucleotidase that hydrolyzes ATP and other nucleotides to regulate extracellular nucleotide levels. Mutations cause autosomal recessive developmental and epileptic encephalopathy with early infantile onset, characterized by severe seizures and developmental delays. The gene is not highly constrained against loss-of-function variants.

OMIMResearchSummary from RefSeq, UniProt
LOEUF 1.60
Clinical SummaryENTPD3
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.
📋
ClinVar Variants
9 unique Pathogenic / Likely Pathogenic· 69 VUS of 89 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.60LOEUF
pLI 0.000
Z-score -0.80
OE 1.17 (0.871.60)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
0.07Z-score
OE missense 0.99 (0.901.09)
285 obs / 288.3 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE1.17 (0.871.60)
00.351.4
Missense OE0.99 (0.901.09)
00.61.4
Synonymous OE0.89
01.21.6
LoF obs/exp: 29 / 24.7Missense obs/exp: 285 / 288.3Syn Z: 0.95

ClinVar Variant Classifications

89 submitted variants in ClinVar

Classification Summary

Pathogenic8
Likely Pathogenic1
VUS69
Likely Benign5
8
Pathogenic
1
Likely Pathogenic
69
VUS
5
Likely Benign

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
0
0
8
0
8
Likely Pathogenic
0
0
1
0
1
VUS
0
69
0
0
69
Likely Benign
0
2
1
2
5
Benign
0
0
0
0
0
Total07110283

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

ENTPD3 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
Open Research Assistant →