ELAC2

Chr 17AR

elaC ribonuclease Z 2

Also known as: COXPD17, ELC2, HPC2

The protein functions as a tRNA 3' processing endoribonuclease that catalyzes the removal of 3' trailers from precursor tRNAs in mitochondria. Biallelic mutations cause combined oxidative phosphorylation deficiency 17 through autosomal recessive inheritance. The pathogenic mechanism involves impaired mitochondrial tRNA processing leading to defective oxidative phosphorylation.

OMIMResearchSummary from RefSeq, OMIM, UniProt
LOFmechanismARLOEUF 1.052 OMIM phenotypes
Clinical SummaryELAC2
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Gene-Disease Validity (ClinGen)
mitochondrial disease · ARDefinitive

Definitive — sufficient evidence for diagnostic panels

Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.
📋
ClinVar Variants
18 unique Pathogenic / Likely Pathogenic· 88 VUS of 300 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.05LOEUF
pLI 0.000
Z-score 1.30
OE 0.79 (0.611.05)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
-0.41Z-score
OE missense 1.05 (0.981.14)
479 obs / 454.4 exp
Tolerant

Tolerant to missense variation

Observed / Expected Ratios
LoF OE0.79 (0.611.05)
00.351.4
Missense OE1.05 (0.981.14)
00.61.4
Synonymous OE1.21
01.21.6
LoF obs/exp: 36 / 45.5Missense obs/exp: 479 / 454.4Syn Z: -2.25

ClinVar Variant Classifications

300 submitted variants in ClinVar

Classification Summary

Pathogenic10
Likely Pathogenic8
VUS88
Likely Benign187
Benign5
Conflicting2
10
Pathogenic
8
Likely Pathogenic
88
VUS
187
Likely Benign
5
Benign
2
Conflicting

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
9
0
1
0
10
Likely Pathogenic
5
3
0
0
8
VUS
1
80
6
1
88
Likely Benign
0
0
96
91
187
Benign
0
1
4
0
5
Conflicting
2
Total158410792300

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

ELAC2 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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