EIF3H

Chr 8

eukaryotic translation initiation factor 3 subunit H

Also known as: EIF3S3, eIF3-gamma, eIF3-p40

The EIF3H protein is a component of the eukaryotic translation initiation factor 3 complex, which is essential for initiating protein synthesis by facilitating ribosome assembly and mRNA recruitment. Mutations in this gene cause autosomal recessive intellectual developmental disorder with seizures, hypotonia, and brain abnormalities, with onset in infancy or early childhood. The gene shows moderate constraint against loss-of-function variants (LOEUF 0.59), and the disorder primarily affects the central nervous system with developmental delays and neurological manifestations.

OMIMResearchSummary from RefSeq, UniProt
DNmechanismLOEUF 0.59
Clinical SummaryEIF3H
Population Constraint (gnomAD)
Constrained for loss-of-function variants (OE-LoF 0.30) despite low pLI — interpret in context.
📋
ClinVar Variants
54 unique Pathogenic / Likely Pathogenic· 57 VUS of 134 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Moderate LoF intolerance
LoF Constraint
0.59LOEUF
pLI 0.047
Z-score 2.90
OE 0.30 (0.160.59)
Moderately constrained

More LoF-intolerant than ~75% of genes

Missense Constraint
0.64Z-score
OE missense 0.87 (0.770.99)
174 obs / 199.4 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.30 (0.160.59)
00.351.4
Missense OE0.87 (0.770.99)
00.61.4
Synonymous OE1.07
01.21.6
LoF obs/exp: 6 / 20.0Missense obs/exp: 174 / 199.4Syn Z: -0.50
DN
0.6647th %ile
GOF
0.4578th %ile
LOF
0.4331th %ile

The highest-scoring mechanism for this gene is dominant-negative.

DNprediction above median

Note: In-silico variant effect predictors (SIFT, PolyPhen, REVEL, CADD) may underestimate pathogenicity of missense variants in genes with GOF or DN mechanisms. Consider functional evidence and clinical context.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

134 submitted variants in ClinVar

Classification Summary

Pathogenic54
VUS57
Likely Benign1
54
Pathogenic
57
VUS
1
Likely Benign

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
0
0
54
0
54
Likely Pathogenic
0
0
0
0
0
VUS
0
43
14
0
57
Likely Benign
0
0
1
0
1
Benign
0
0
0
0
0
Total043690112

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

EIF3H · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
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