ECI1

Chr 16

enoyl-CoA delta isomerase 1

Also known as: DCI

The protein is a key mitochondrial enzyme that catalyzes the isomerization of 3-cis and 3-trans-enoyl-CoA esters to 2-trans-enoyl-CoA intermediates during beta-oxidation of unsaturated fatty acids. Mutations cause autosomal recessive defects in fatty acid oxidation leading to metabolic dysfunction. The gene shows very low constraint against loss-of-function variants (extremely low pLI score), consistent with recessive inheritance patterns.

OMIMResearchSummary from RefSeq, UniProt
DNmechanismLOEUF 1.84
Clinical SummaryECI1
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.84LOEUF
pLI 0.000
Z-score -0.95
OE 1.29 (0.871.84)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
-0.42Z-score
OE missense 1.09 (0.971.23)
192 obs / 176.2 exp
Tolerant

Tolerant to missense variation

Observed / Expected Ratios
LoF OE1.29 (0.871.84)
00.351.4
Missense OE1.09 (0.971.23)
00.61.4
Synonymous OE1.08
01.21.6
LoF obs/exp: 16 / 12.4Missense obs/exp: 192 / 176.2Syn Z: -0.57
DN
0.6746th %ile
GOF
0.5562th %ile
LOF
0.3745th %ile

The highest-scoring mechanism for this gene is dominant-negative.

DNprediction above median

Note: In-silico variant effect predictors (SIFT, PolyPhen, REVEL, CADD) may underestimate pathogenicity of missense variants in genes with GOF or DN mechanisms. Consider functional evidence and clinical context.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

ECI1 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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