EBP

Chr XXLDXLR

EBP cholestenol delta-isomerase

Also known as: CDPX2, CHO2, CPX, CPXD, D8D7I, MEND

EBP encodes an isomerase that catalyzes the conversion of Delta(8)-sterols to their corresponding Delta(7)-isomers in the cholesterol biosynthesis pathway. Mutations cause X-linked chondrodysplasia punctata type 2 (Conradi-Hünermann syndrome) and MEND syndrome, skeletal disorders characterized by stippled cartilage calcifications and limb abnormalities. The gene shows X-linked dominant inheritance and is highly constrained against loss-of-function variants (pLI 0.94, LOEUF 0.34).

GeneReviewsOMIMResearchSummary from RefSeq, OMIM, UniProt
LOFmechanismXLD/XLRLOEUF 0.342 OMIM phenotypes
Clinical SummaryEBP
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Gene-Disease Validity (ClinGen)
MEND syndrome · XLDefinitive

Definitive — sufficient evidence for diagnostic panels

Population Constraint (gnomAD)
Highly constrained gene — heterozygous loss-of-function variants are very rare in the population (pLI 0.94). One damaged copy is likely sufficient to cause disease.
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Clinical Trials
2 active or recruiting trials — potential therapeutic options may be available
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GeneReview available — EBP
Authoritative clinical overview · Recommended first read
Open GeneReview ↗

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

LoF intolerant — likely haploinsufficient
LoF Constraint
0.34LOEUF
pLI 0.936
Z-score 2.74
OE 0.00 (0.000.34)
Highly constrained

Highly LoF-intolerant (top ~10% of genes)

Missense Constraint
1.49Z-score
OE missense 0.57 (0.460.71)
55 obs / 96.3 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.00 (0.000.34)
00.351.4
Missense OE0.57 (0.460.71)
00.61.4
Synonymous OE0.99
01.21.6
LoF obs/exp: 0 / 8.8Missense obs/exp: 55 / 96.3Syn Z: 0.06

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

EBP · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold
Clinical Literature
Open Research Assistant →
Key Publications
Landmark & review papers · by relevance
PubMed
Top 5 results · since 2015Search PubMed ↗