DZIP1

Chr 13ADAR

DAZ interacting zinc finger protein 1

Also known as: DZIP, DZIPt1, MMVP3, MVP3, SPGF47

DZIP1 encodes a molecular adapter that recruits protein complexes required for cilium assembly and function to the cilium basal body, and activates vesicle-mediated transport of proteins to the cilium. Mutations cause mitral valve prolapse and spermatogenic failure in males, with both autosomal dominant and autosomal recessive inheritance patterns reported. The gene is not constrained against loss-of-function variants, and the associated phenotypes reflect the protein's essential roles in cardiac development and sperm flagellum assembly through ciliogenesis.

OMIMResearchSummary from RefSeq, OMIM, UniProt
AD/ARLOEUF 1.032 OMIM phenotypes
Clinical SummaryDZIP1
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.
📋
ClinVar Variants
83 unique Pathogenic / Likely Pathogenic· 123 VUS of 229 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.03LOEUF
pLI 0.000
Z-score 1.39
OE 0.78 (0.601.03)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
0.95Z-score
OE missense 0.88 (0.810.95)
421 obs / 479.8 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.78 (0.601.03)
00.351.4
Missense OE0.88 (0.810.95)
00.61.4
Synonymous OE0.95
01.21.6
LoF obs/exp: 36 / 46.2Missense obs/exp: 421 / 479.8Syn Z: 0.53

ClinVar Variant Classifications

229 submitted variants in ClinVar

Classification Summary

Pathogenic81
Likely Pathogenic2
VUS123
Likely Benign4
Benign3
81
Pathogenic
2
Likely Pathogenic
123
VUS
4
Likely Benign
3
Benign

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
1
1
79
0
81
Likely Pathogenic
2
0
0
0
2
VUS
0
113
10
0
123
Likely Benign
0
4
0
0
4
Benign
0
2
0
1
3
Total3120891213

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

DZIP1 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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