DSCAML1

Chr 11

DS cell adhesion molecule like 1

Also known as: DSCAM2

DSCAML1 encodes a cell adhesion molecule that promotes neuronal self-avoidance by mediating repulsion between neuronal processes of the same cell or cell type, and facilitates lamina-specific synaptic connections in the retina. Mutations cause autosomal dominant or recessive intellectual disability and developmental delay, with some patients showing additional features including autism spectrum disorder and seizures. This gene is highly constrained against loss-of-function variants, indicating that such mutations are likely to have significant clinical consequences.

OMIMResearchSummary from RefSeq, UniProt
LOFmechanismLOEUF 0.17
Clinical SummaryDSCAML1
Population Constraint (gnomAD)
Highly constrained gene — heterozygous loss-of-function variants are very rare in the population (pLI 1.00). One damaged copy is likely sufficient to cause disease.

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Dual constrained — LoF & missense intolerant
LoF Constraint
0.17LOEUF
pLI 1.000
Z-score 7.88
OE 0.09 (0.050.17)
Highly constrained

Highly LoF-intolerant (top ~10% of genes)

Missense Constraint
3.15Z-score
OE missense 0.76 (0.720.80)
1030 obs / 1356.5 exp
Constrained

Highly missense-constrained (top ~0.1%)

Observed / Expected Ratios
LoF OE0.09 (0.050.17)
00.351.4
Missense OE0.76 (0.720.80)
00.61.4
Synonymous OE1.11
01.21.6
LoF obs/exp: 8 / 87.6Missense obs/exp: 1030 / 1356.5Syn Z: -2.05
Curated Mechanism (G2P)Gene2Phenotype (DDG2P) ↗
limitedDSCAML1-related retinitis pigmentosaOTHERAR

Predictions shown for reference only — model trained on dominant genes, not applicable to AR conditions.

DN
0.5280th %ile
GOF
0.5562th %ile
LOF
0.68top 25%

The Badonyi & Marsh prediction model was trained exclusively on dominant disease genes. Predictions are not reliable for genes with autosomal recessive inheritance and are shown at reduced opacity for reference only.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312. Mechanism ranking also informed by gnomAD constraint, ClinVar, and ClinGen data.

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

DSCAML1 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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Full-Text Mentions
NLP-detected gene mentions in article bodies · via PubTator3
PubTator3
Top 3 full-text resultsSearch PubTator3 ↗
Recent Gene-Specific Literature
Gene in title · MEDLINE · newest first
Europe PMC