DPAGT1

Chr 11AR

dolichyl-phosphate N-acetylglucosaminephosphotransferase 1

Also known as: ALG7, CDG-Ij, CDG1J, CMS13, CMSTA2, D11S366, DGPT, DPAGT

The encoded enzyme catalyzes the first step in the dolichol-linked oligosaccharide pathway for glycoprotein biosynthesis as an integral endoplasmic reticulum membrane protein. Autosomal recessive mutations cause congenital disorder of glycosylation type Ij and congenital myasthenic syndrome 13 with tubular aggregates. The pathogenic mechanism appears to be dominant-negative, where mutant proteins interfere with normal glycosylation processes.

OMIMResearchSummary from RefSeq, OMIM, UniProt, Mechanism
LOFmechanismARLOEUF 1.082 OMIM phenotypes
Clinical SummaryDPAGT1
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Gene-Disease Validity (ClinGen)
DPAGT1-congenital disorder of glycosylation · ARDefinitive

Definitive — sufficient evidence for diagnostic panels

Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
1.08LOEUF
pLI 0.000
Z-score 1.33
OE 0.64 (0.391.08)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint
1.43Z-score
OE missense 0.73 (0.640.83)
156 obs / 214.8 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.64 (0.391.08)
00.351.4
Missense OE0.73 (0.640.83)
00.61.4
Synonymous OE0.85
01.21.6
LoF obs/exp: 10 / 15.7Missense obs/exp: 156 / 214.8Syn Z: 1.14
Curated Mechanism (G2P)Gene2Phenotype (DDG2P) ↗
definitiveDPAGT1-related congenital disorder of glycosylationOTHERAR
definitiveDPAGT1-related myasthenic syndrome, congenital, with tubular aggregatesLOFAR

Predictions shown for reference only — model trained on dominant genes, not applicable to AR conditions.

DN
0.83top 10%
GOF
0.6540th %ile
LOF
0.1796th %ile

The Badonyi & Marsh prediction model was trained exclusively on dominant disease genes. Predictions are not reliable for genes with autosomal recessive inheritance and are shown at reduced opacity for reference only.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

DPAGT1 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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