DOCK11

Chr XXLR

dedicator of cytokinesis 11

Also known as: ACG, ADMIDX, ZIZ2, bB128O4.1

DOCK11 encodes a guanine nucleotide-exchange factor that activates CDC42 and is required for marginal zone B-cell development and filopodia formation. Mutations cause X-linked recessive autoinflammatory disease with multisystem immune dysregulation. The gene is highly constrained against loss-of-function variants (LOEUF 0.37), indicating that complete loss of function is likely pathogenic.

OMIMResearchSummary from RefSeq, OMIM, UniProt
XLRLOEUF 0.371 OMIM phenotype
Clinical SummaryDOCK11
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Gene-Disease Validity (ClinGen)
autoinflammatory disease, multisystem, with immune dysregulation, X-linked · XLStrong

Strong evidence — appropriate for clinical testing

Population Constraint (gnomAD)
Constrained for loss-of-function variants (OE-LoF 0.26) despite low pLI — interpret in context.
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ClinVar Variants
200 total variants — no pathogenic classifications of 200 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Moderate LoF intolerance
LoF Constraint
0.37LOEUF
pLI 0.012
Z-score 6.08
OE 0.26 (0.180.37)
Moderately constrained

More LoF-intolerant than ~75% of genes

Missense Constraint
2.68Z-score
OE missense 0.72 (0.670.77)
519 obs / 722.0 exp
Mild constraint

Moderately missense-constrained (top ~2.5%)

Observed / Expected Ratios
LoF OE0.26 (0.180.37)
00.351.4
Missense OE0.72 (0.670.77)
00.61.4
Synonymous OE0.94
01.21.6
LoF obs/exp: 20 / 78.0Missense obs/exp: 519 / 722.0Syn Z: 0.73

ClinVar Variant Classifications

200 submitted variants in ClinVar

Classification Summary

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories· variant type breakdown unavailable

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
0
Likely Pathogenic
0
VUS
0
Likely Benign
0
Benign
0
Total0

Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

DOCK11 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →
Clinical Literature
Open Research Assistant →
Key Publications
Landmark & review papers · by relevance
PubMed
Top 5 results · since 2015Search PubMed ↗