DENND3

Chr 8

DENN domain containing 3

The DENND3 protein functions as a guanine nucleotide exchange factor that activates RAB12, regulating autophagy in response to starvation and controlling protein transport from recycling endosomes to lysosomes. Mutations cause neurodevelopmental disorders with intellectual disability, though the inheritance pattern has not been clearly established. The gene shows minimal constraint against loss-of-function variants (very low pLI score), suggesting tolerance to complete protein loss.

Summary from RefSeq, UniProt
Research Assistant →
0
Active trials
5
Pubs (1 yr)
56
P/LP submissions
0%
P/LP missense
0.66
LOEUF
Mechanism
Clinical SummaryDENND3
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.
📋
ClinVar Variants
56 unique Pathogenic / Likely Pathogenic· 172 VUS of 290 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
0.66LOEUF
pLI 0.000
Z-score 3.65
OE 0.48 (0.360.66)
Tolerant

Typical tolerance to LoF variation

Missense Constraint
2.37Z-score
OE missense 0.75 (0.700.81)
556 obs / 736.7 exp
Mild constraint

Moderately missense-constrained (top ~2.5%)

Observed / Expected Ratios
LoF OE0.48 (0.360.66)
00.351.4
Missense OE0.75 (0.700.81)
00.61.4
Synonymous OE0.99
01.21.6
LoF obs/exp: 28 / 58.0Missense obs/exp: 556 / 736.7Syn Z: 0.18

ClinVar Variant Classifications

290 submitted variants in ClinVar

Classification Summary

Pathogenic52
Likely Pathogenic4
VUS172
Likely Benign16
Benign12
Conflicting1
52
Pathogenic
4
Likely Pathogenic
172
VUS
16
Likely Benign
12
Benign
1
Conflicting

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
0
0
52
0
52
Likely Pathogenic
1
0
3
0
4
VUS
0
167
3
2
172
Likely Benign
0
14
0
2
16
Benign
0
3
3
6
12
Conflicting
1
Total11846110257

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

DENND3 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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