DDX11

Chr 12AR

DEAD/H-box helicase 11

Also known as: CHL1, CHLR1, KRG2, WABS

DDX11 encodes a DNA helicase with ATPase activity that maintains genomic stability during DNA replication, repair, and chromosome segregation, and also participates in ribosomal RNA synthesis. Biallelic mutations cause Warsaw breakage syndrome, an autosomal recessive disorder characterized by growth retardation, microcephaly, hearing loss, and chromosomal instability with a high frequency of sister chromatid exchanges. The gene shows very low constraint against loss-of-function variants (pLI near zero), which is consistent with its recessive inheritance pattern.

OMIMResearchSummary from RefSeq, OMIM, UniProt
LOFmechanismARLOEUF 0.961 OMIM phenotype
Clinical SummaryDDX11
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Gene-Disease Validity (ClinGen)
Warsaw breakage syndrome · ARDefinitive

Definitive — sufficient evidence for diagnostic panels

Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
0.96LOEUF
pLI 0.000
Z-score 1.79
OE 0.74 (0.570.96)
Tolerant

Typical tolerance to LoF variation

Missense Constraint
-0.22Z-score
OE missense 1.03 (0.961.10)
573 obs / 558.3 exp
Tolerant

Tolerant to missense variation

Observed / Expected Ratios
LoF OE0.74 (0.570.96)
00.351.4
Missense OE1.03 (0.961.10)
00.61.4
Synonymous OE0.98
01.21.6
LoF obs/exp: 40 / 54.2Missense obs/exp: 573 / 558.3Syn Z: 0.18

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

DDX11 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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