CPEB2

Chr 4

cytoplasmic polyadenylation element binding protein 2

Also known as: CPE-BP2, CPEB-2, hCPEB-2

CPEB2 encodes a cytoplasmic polyadenylation element binding protein that regulates mRNA translation and is required for cell cycle progression from metaphase to anaphase. Mutations cause autosomal recessive developmental and epileptic encephalopathy with onset in infancy, characterized by severe intellectual disability, seizures, and brain malformations. The gene is highly constrained against loss-of-function variants in the general population.

Summary from RefSeq, UniProt
Research Assistant →
0
Active trials
12
Pubs (1 yr)
55
P/LP submissions
0%
P/LP missense
0.59
LOEUF
Mechanism
Clinical SummaryCPEB2
Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.
📋
ClinVar Variants
55 unique Pathogenic / Likely Pathogenic· 223 VUS of 295 total submissions

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Moderate LoF intolerance
LoF Constraint
0.59LOEUF
pLI 0.000
Z-score 3.45
OE 0.37 (0.240.59)
Moderately constrained

More LoF-intolerant than ~75% of genes

Missense Constraint
0.68Z-score
OE missense 0.91 (0.830.99)
389 obs / 428.4 exp
Tolerant

Mild missense constraint

Observed / Expected Ratios
LoF OE0.37 (0.240.59)
00.351.4
Missense OE0.91 (0.830.99)
00.61.4
Synonymous OE1.27
01.21.6
LoF obs/exp: 13 / 35.1Missense obs/exp: 389 / 428.4Syn Z: -2.65

ClinVar Variant Classifications

295 submitted variants in ClinVar

Classification Summary

Pathogenic52
Likely Pathogenic3
VUS223
Likely Benign1
Benign1
52
Pathogenic
3
Likely Pathogenic
223
VUS
1
Likely Benign
1
Benign

Curated Variants Distribution

Classified variants from ClinVar · 5 ACMG categories

ClassificationLoFMissense + InframeNon-codingSynonymousTotal
Pathogenic
0
0
52
0
52
Likely Pathogenic
0
0
3
0
3
VUS
0
221
2
0
223
Likely Benign
0
0
0
1
1
Benign
0
0
1
0
1
Total0221581280

LoF = frameshift, stop gained/lost, canonical splice · Counts from ClinVar esearch · Updated hourly

View in ClinVar →

Protein Context — Lollipop Plot

CPEB2 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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