COX6A1

Chr 12AR

cytochrome c oxidase subunit 6A1

Also known as: CMTRID, COX6A, COX6AL

Cytochrome c oxidase (COX), the terminal enzyme of the mitochondrial respiratory chain, catalyzes the electron transfer from reduced cytochrome c to oxygen. It is a heteromeric complex consisting of 3 catalytic subunits encoded by mitochondrial genes and multiple structural subunits encoded by nuclear genes. The mitochondrially-encoded subunits function in the electron transfer and the nuclear-encoded subunits may function in the regulation and assembly of the complex. This nuclear gene encodes polypeptide 1 (liver isoform) of subunit VIa, and polypeptide 1 is found in all non-muscle tissues. Polypeptide 2 (heart/muscle isoform) of subunit VIa is encoded by a different gene, and is present only in striated muscles. These two polypeptides share 66% amino acid sequence identity. It has been reported that there may be several pseudogenes on chromosomes 1, 6, 7q21, 7q31-32 and 12. However, only one pseudogene (COX6A1P) on chromosome 1p31.1 has been documented. [provided by RefSeq, Jul 2008]

OMIMResearchGenerating clinical summary…

Primary Disease Associations & Inheritance

Charcot-Marie-Tooth disease, recessive intermediate DMIM #616039
AR

Clinical highlights

Gene-disease validity (ClinGen)
mitochondrial disease · ARStrongappropriate for clinical testing
0
Active trials
10
Pubs (1 yr)
P/LP submissions
P/LP missense
1.76
LOEUF
Multiple*
Mechanism· predicted

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint?
1.76LOEUF
pLI 0.002
Z-score 0.25
OE 0.88 (0.421.76)
Tolerant

Highly tolerant — LoF variants common in population

Missense Constraint?
-1.42Z-score
OE missense 1.49 (1.261.76)
99 obs / 66.5 exp
Tolerant

Tolerant to missense variation

Observed / Expected Ratios?
LoF OE?0.88 (0.421.76)
00.351.4
Missense OE?1.49 (1.261.76)
00.61.4
Synonymous OE?1.46
01.21.6
LoF obs/exp: 4 / 4.6Missense obs/exp: 99 / 66.5Syn Z: -1.93

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

COX6A1 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

Search ClinicalTrials.gov →