COQ2

Chr 4

coenzyme Q2, polyprenyltransferase

Also known as: CL640, COQ10D1, MSA1, PHB:PPT

COQ2 encodes an enzyme that catalyzes the prenylation of para-hydroxybenzoate in the biosynthesis of coenzyme Q10, which functions as an electron carrier in the mitochondrial respiratory chain and as a lipid-soluble antioxidant. Mutations cause primary coenzyme Q10 deficiency, a mitochondrial disorder that can present as encephalomyopathy or nephropathy with primary renal involvement. The gene shows both autosomal recessive and autosomal dominant inheritance patterns.

GeneReviewsResearchSummary from RefSeq, OMIM, UniProt
LOFmechanismLOEUF 0.89
Clinical SummaryCOQ2
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Gene-Disease Validity (ClinGen)
mitochondrial disease · ARDefinitive

Definitive — sufficient evidence for diagnostic panels

Population Constraint (gnomAD)
Low constraint (pLI 0.00) — loss-of-function variants are relatively tolerated in the population.
📖
GeneReview available — COQ2
Authoritative clinical overview · Recommended first read
Open GeneReview ↗
Some data sources returned errors (1)

omim: Error: OMIM fetch failed: 429

Population Genetics & Constraint

gnomAD v4 — loss-of-function & missense intolerance

Tolerant — LoF & missense variants common in population
LoF Constraint
0.89LOEUF
pLI 0.001
Z-score 1.88
OE 0.47 (0.270.89)
Tolerant

Typical tolerance to LoF variation

Missense Constraint
-0.03Z-score
OE missense 1.01 (0.891.13)
194 obs / 192.9 exp
Tolerant

Tolerant to missense variation

Observed / Expected Ratios
LoF OE0.47 (0.270.89)
00.351.4
Missense OE1.01 (0.891.13)
00.61.4
Synonymous OE1.18
01.21.6
LoF obs/exp: 7 / 14.8Missense obs/exp: 194 / 192.9Syn Z: -1.21
Curated Mechanism (G2P)Gene2Phenotype (DDG2P) ↗
definitiveCOQ2-related coenzyme Q10 deficiencyLOFAR

Predictions shown for reference only — model trained on dominant genes, not applicable to AR conditions.

DN
0.77top 25%
GOF
0.5954th %ile
LOF
0.3066th %ile

The Badonyi & Marsh prediction model was trained exclusively on dominant disease genes. Predictions are not reliable for genes with autosomal recessive inheritance and are shown at reduced opacity for reference only.

Predictions from Badonyi M, Marsh JA. PLoS ONE. 2024;19(8):e0307312.

ClinVar Variant Classifications

0 submitted variants in ClinVar

Protein Context — Lollipop Plot

COQ2 · protein map & ClinVar variants

Showing all ClinVar variants across the protein. Search a specific variant to highlight its position.

3D Protein StructureAlphaFold

Clinical Trials

Active and recruiting trials from ClinicalTrials.gov

No active trials found for this gene.

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Clinical Literature
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